Genetic variation in the alternative splicing regulator RBM20 is associated with dilated cardiomyopathy

Heart Rhythm. 2012 Mar;9(3):390-6. doi: 10.1016/j.hrthm.2011.10.016. Epub 2011 Oct 17.

Abstract

Background: Dilated cardiomyopathy (DCM) is a leading cause of heart failure and death. The etiology of DCM is genetically heterogeneous.

Objectives: We sought to define the prevalence of mutations in the RNA splicing protein RBM20 in a large cohort with DCM and to determine whether genetic variation in RBM20 is associated with clinical outcomes.

Methods: Subjects included in the Genetic Risk Assessment of Defibrillator Events (GRADE) study were aged at least 18 years, had an ejection fraction of ≤30%, and an implantable cardioverter-defibrillator (ICD). The coding region and splice junctions of RBM20 were screened in subjects with DCM; 2 common polymorphisms in RBM20, rs942077 and rs35141404, were genotyped in all GRADE subjects.

Results: A total of 1465 subjects were enrolled in the GRADE study, and 283 with DCM were screened for RBM20 mutations. The mean age of subjects with DCM was 58 ± 13 years, 64% were males, and the mean follow-up time was 24.2 ± 17.1 months after ICD placement. RBM20 mutations were identified in 8 subjects with DCM (2.8%). Mutation carriers had a similar survival, transplantation rate, and frequency of ICD therapy compared with nonmutation carriers. Three of 8 subjects with RBM20 mutations (37.5%) had atrial fibrillation (AF), whereas 19 subjects without mutations (7.4%) had AF (P = .02). Among all GRADE subjects, rs35141404 was associated with AF (minor allele odds ratio = 0.62; 95% confidence interval = 0.44-0.86; P = .006). In the subset of GRADE subjects with DCM, rs35141404 was associated with AF (minor allele odds ratio = 0.58; P = .047).

Conclusions: Mutations in RBM20 were observed in approximately 3% of subjects with DCM. There were no differences in survival, transplantation rate, and frequency of ICD therapy in mutation carriers.

MeSH terms

  • Adult
  • Aged
  • Alternative Splicing / genetics
  • Arrhythmias, Cardiac* / epidemiology
  • Arrhythmias, Cardiac* / etiology
  • Arrhythmias, Cardiac* / genetics
  • Arrhythmias, Cardiac* / therapy
  • Cardiac Pacing, Artificial / methods*
  • Cardiomyopathy, Dilated* / complications
  • Cardiomyopathy, Dilated* / diagnosis
  • Cardiomyopathy, Dilated* / genetics
  • Cardiomyopathy, Dilated* / mortality
  • Cardiomyopathy, Dilated* / therapy
  • Defibrillators, Implantable
  • Female
  • Heart Transplantation / statistics & numerical data*
  • Humans
  • Male
  • Middle Aged
  • Mutation, Missense
  • Polymorphism, Single Nucleotide
  • Prevalence
  • RNA Splice Sites / genetics
  • RNA-Binding Proteins / genetics*
  • Risk Assessment
  • Stroke Volume
  • Survival Rate
  • United States / epidemiology

Substances

  • RNA Splice Sites
  • RNA-Binding Proteins
  • ribonucleic acid binding motif protein 20, human