Inflammatory bowel disease manifesting after surgical treatment for Hirschsprung disease

J Pediatr Gastroenterol Nutr. 2012 Sep;55(3):272-7. doi: 10.1097/MPG.0b013e31824f617a.

Abstract

Eight children developed chronic inflammatory bowel disease (IBD) 4 to 21 years after surgery for Hirschsprung disease. Three had trisomy 21 and 6 experienced chronic or recurrent enterocolitis. Four had a family history of IBD. Clinical presentation included chronic diarrhea, hematochezia, abscess, and fistula formation. Three required surgery for fistula, stricture, and small bowel obstruction and the other 5 were managed medically. Recognition of this condition may be important in the long-term follow-up of children with Hirschsprung disease, and patients who have carried a diagnosis of chronic enterocolitis may warrant further investigation looking for evidence of IBD.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Abscess / etiology
  • Adolescent
  • Child
  • Child, Preschool
  • Chronic Disease
  • Diarrhea / etiology
  • Down Syndrome
  • Enterocolitis* / etiology
  • Female
  • Fistula / etiology
  • Fistula / surgery
  • Gastrointestinal Hemorrhage / etiology
  • Hirschsprung Disease* / complications
  • Hirschsprung Disease* / surgery
  • Humans
  • Infant
  • Infant, Newborn
  • Inflammatory Bowel Diseases* / etiology
  • Intestinal Obstruction / etiology
  • Intestine, Small / pathology
  • Male