[Molecular diagnosis of Gaucher disease in Tunisia]

Pathol Biol (Paris). 2013 Apr;61(2):59-63. doi: 10.1016/j.patbio.2012.03.006. Epub 2012 Apr 27.
[Article in French]

Abstract

Gaucher disease is a lysosomal storage disorder caused by a deficiency of the enzyme acid β-glucosidase. In order to determine the mutation spectrum in Tunisia, we performed recurrent mutation screening in 30 Tunisian patients with Gaucher disease. Screening of recurrent mutation by PCR/RFLP and direct sequencing had shown that N370S was the most frequent mutation (22/50 mutant alleles, 44%), followed by L444P mutation, which is found in 16% (8/50 mutant alleles). The recombinant allele (RecNciI) represented 14%. Our findings revealed that the genotype N370S/RecNciI was mosst frequent in patients with childhood onset and it was associated with severe visceral involvement. The screening of these three mutations provided a simple tool for molecular diagnosis of Gaucher disease in Tunisian patients and allowed also genetic counselling for their family members.

Publication types

  • English Abstract

MeSH terms

  • Adolescent
  • Adult
  • Age of Onset
  • Child
  • Child, Preschool
  • DNA Mutational Analysis / methods
  • Female
  • Gaucher Disease / complications
  • Gaucher Disease / diagnosis*
  • Gaucher Disease / epidemiology
  • Gaucher Disease / genetics*
  • Genetic Predisposition to Disease
  • Genotype
  • Glucosylceramidase / genetics
  • Humans
  • Infant
  • Infant, Newborn
  • Male
  • Middle Aged
  • Molecular Diagnostic Techniques*
  • Polymerase Chain Reaction / methods
  • Polymorphism, Restriction Fragment Length / physiology
  • Tunisia / epidemiology
  • Young Adult

Substances

  • Glucosylceramidase