Three patients with Wolf-Hirschhorn syndrome carrying a satellited chromosome 4p

Birth Defects Res A Clin Mol Teratol. 2012 Jul;94(7):549-52. doi: 10.1002/bdra.23019. Epub 2012 May 29.

Abstract

Background: Wolf-Hirschhorn syndrome (WHS) is caused by a deletion involving the 4p16.3 region. Approximately 70% of WHS patients have a de novo isolated deletion and 22% involve unbalanced translocations. However, WHS with unbalanced rearrangements involving the short arm of an acrocentric chromosome are infrequently reported.

Methods: Cytogenetic and molecular analyses by using standard G-banding, argyrophilic nucleolar organiser region (Ag-NOR) staining, fluorescence in situ hybridization, and single nucleotide polymorphism array for copy number detection were performed in three patients with WHS phenotype from two Chinese families.

Results: A heterozygous 2,767,380-bp terminal 4p deletion was detected in patients 1 and 2 and a heterozygous 5,047,291-bp terminal 4p deletion was detected in patient3. Clinical comparisons among our patients and previously reported cases have been reviewed.

Conclusion: Two terminal 4p deletions were identified in three WHS patients with a satellited 4p and an attempt was made to refine the genotypic-phenotypic correlations of the deleted regions.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Child
  • Child, Preschool
  • Chromosomes, Human, Pair 4 / genetics*
  • Female
  • Genotype
  • Heterozygote
  • Humans
  • In Situ Hybridization, Fluorescence
  • Male
  • Phenotype
  • Translocation, Genetic
  • Wolf-Hirschhorn Syndrome / genetics*