Bannayan-Riley-Ruvalcaba syndrome with progressive spinal epidural lipomatosis

Neuropediatrics. 2012 Aug;43(4):221-4. doi: 10.1055/s-0032-1324402. Epub 2012 Aug 21.

Abstract

We present a case study of an 11-year-old boy with Bannayan-Riley-Ruvalcaba syndrome (BRRS) with macrocephaly, lipomatosis, and penile freckles. BRRS was confirmed by a germline mutation in the phosphatase and tensin homolog (PTEN) gene. Repeated spinal imaging demonstrated an extensive progressive spinal epidural lipomatosis, compressing and dislocating the dural sac, so far without neurological deficits. Patients with BRRS are probably a risk for progressive spinal epidural lipomatosis and should be carefully monitored by neurological examinations and eventually neuroimaging follow-up studies.

Publication types

  • Case Reports

MeSH terms

  • Child, Preschool
  • Epidural Space / pathology
  • Follow-Up Studies
  • Hamartoma Syndrome, Multiple / complications*
  • Hamartoma Syndrome, Multiple / genetics
  • Humans
  • Karyotyping
  • Lipomatosis / complications*
  • Lipomatosis / genetics
  • Magnetic Resonance Imaging
  • Male
  • PTEN Phosphohydrolase / genetics
  • Spinal Cord / pathology
  • Spinal Neoplasms / complications*
  • Spinal Neoplasms / genetics

Substances

  • PTEN Phosphohydrolase