Atypical findings in three patients with Pai syndrome and literature review

Am J Med Genet A. 2012 Nov;158A(11):2899-904. doi: 10.1002/ajmg.a.35592. Epub 2012 Sep 17.

Abstract

Pai syndrome is a rare disorder characterized by congenital nasal or facial polyp, midline cleft lip, pericallosal lipoma, ocular anomalies, and normal neuropsychological development. Here, we report on three patients with Pai syndrome and atypical findings: temporal triangular alopecia, posterior lenticonus, bilateral palatal pits, bifid uvula, hypospadias, sacral dimple, true tracheal bronchus, and epilepsy. Thirty-three cases of Pai syndrome have been described so far. We present a review of the previously reported cases and suggest modified diagnostic criteria for Pai syndrome.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't
  • Review

MeSH terms

  • Agenesis of Corpus Callosum / diagnosis*
  • Brain / pathology
  • Child
  • Cleft Lip / diagnosis*
  • Coloboma / diagnosis*
  • Facies
  • Female
  • Humans
  • Infant, Newborn
  • Lipoma / diagnosis*
  • Magnetic Resonance Imaging
  • Male
  • Nasal Polyps / diagnosis*
  • Phenotype
  • Skin Diseases / diagnosis*

Supplementary concepts

  • Median cleft lip, corpus callosum, lipoma, and skin polyps