Profiling sirolimus-induced inflammatory syndrome: a prospective tricentric observational study

PLoS One. 2013;8(1):e53078. doi: 10.1371/journal.pone.0053078. Epub 2013 Jan 7.

Abstract

Background: The use of the immunosuppressant sirolimus in kidney transplantation has been made problematic by the frequent occurrence of various side effects, including paradoxical inflammatory manifestations, the pathophysiology of which has remained elusive.

Methods: 30 kidney transplant recipients that required a switch from calcineurin inhibitor to sirolimus-based immunosuppression, were prospectively followed for 3 months. Inflammatory symptoms were quantified by the patients using visual analogue scales and serum samples were collected before, 15, 30, and 90 days after the switch.

Results: 66% of patients reported at least 1 inflammatory symptom, cutaneo-mucosal manifestations being the most frequent. Inflammatory symptoms were characterized by their lability and stochastic nature, each patient exhibiting a unique clinical presentation. The biochemical profile was more uniform with a drop of hemoglobin and a concomitant rise of inflammatory acute phase proteins, which peaked in the serum 1 month after the switch. Analyzing the impact of sirolimus introduction on cytokine microenvironment, we observed an increase of IL6 and TNFα without compensation of the negative feedback loops dependent on IL10 and soluble TNF receptors. IL6 and TNFα changes correlated with the intensity of biochemical and clinical inflammatory manifestations in a linear regression model.

Conclusions: Sirolimus triggers a destabilization of the inflammatory cytokine balance in transplanted patients that promotes a paradoxical inflammatory response with mild stochastic clinical symptoms in the weeks following drug introduction. This pathophysiologic mechanism unifies the various individual inflammatory side effects recurrently reported with sirolimus suggesting that they should be considered as a single syndromic entity.

Publication types

  • Clinical Trial
  • Multicenter Study
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Aged
  • Calcineurin Inhibitors
  • Cytochrome P-450 CYP3A / genetics
  • Female
  • Genotype
  • Humans
  • Immunosuppressive Agents / adverse effects*
  • Immunosuppressive Agents / immunology
  • Inflammation / chemically induced
  • Interleukin-10 / blood
  • Interleukin-10 / immunology
  • Interleukin-6 / blood
  • Interleukin-6 / immunology
  • Kidney Transplantation* / adverse effects
  • Male
  • Middle Aged
  • Prospective Studies
  • Sirolimus / adverse effects*
  • Sirolimus / immunology
  • Tumor Necrosis Factor-alpha / blood
  • Tumor Necrosis Factor-alpha / immunology

Substances

  • Calcineurin Inhibitors
  • Immunosuppressive Agents
  • Interleukin-6
  • Tumor Necrosis Factor-alpha
  • Interleukin-10
  • CYP3A5 protein, human
  • Cytochrome P-450 CYP3A
  • Sirolimus

Grants and funding

SIRILYGRE study was supported by an educational grant from Wyeth Laboratory. The funder had no role in study design, data collection and analysis, decision to publish, or preparation of the manuscript.