Rabson-Mendenhall syndrome with recurrent cerebral infarcts caused by a novel INSR mutation

Int J Dermatol. 2013 Feb;52(2):182-5. doi: 10.1111/j.1365-4632.2012.05665.x.

Abstract

Rabson-Mendenhall syndrome (RMS) is an autosomal recessive disorder characterized by extreme insulin resistance and certain characteristic phenotypic features. The primary defect lies in the insulin receptor and involves biallelic mutations that lead to a loss of function through various postulated defects. We present a 9-year-old female patient with RMS complicated by multiple cerebral infarcts, in whom genetic analysis revealed a novel insulin receptor mutation.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Acanthosis Nigricans / genetics*
  • Cerebral Infarction / genetics*
  • Child
  • Clitoris / abnormalities
  • Dentofacial Deformities / genetics*
  • Donohue Syndrome / genetics*
  • Female
  • Genes, Recessive
  • Humans
  • Phenotype
  • Receptor, Insulin / genetics*
  • Recurrence

Substances

  • Receptor, Insulin