Control of AA amyloidosis complicating Crohn's disease: a clinico-pathological study

Eur J Clin Invest. 2013 Mar;43(3):292-301. doi: 10.1111/eci.12045. Epub 2013 Feb 4.

Abstract

Background: Immunosuppressive drugs may prevent or partially reverse progression of renal AA-amyloidosis, a rare complication of Crohn's disease, often fatal due to renal failure.

Materials and methods: The clinical, biological and pathological data of 16 patients treated since 1976 were reviewed. Serum amyloid A was determined in surviving patients.

Results: The median age of the 16 patients (13 men) was 23·5 years (range 16-69). At Crohn's disease onset, Montreal phenotypes were similar to reported data. Out of 15 patients with renal insufficiency, 8 developed a nephrotic syndrome and 7 a low grade proteinuria. The single patient without renal insufficiency had nephrotic syndrome. A significant correlation (P < 0·05) between the extension of renal amyloid A and sclerosis was found in 12 patients. One patient had a 10 year remission of nephrotic syndrome with immunosuppressive drugs. In 6 patients treated with anti-TNF-α (Tumor-Necrosis-Factor-α) agents, anaphylactic reaction (1/6), death from septic shock (1/6), 5-year remission (1/6) or reduction of nephrotic syndrome (1/6) and stabilization of renal insufficiency (2/6) were observed. Surgery was performed in 10 patients. Kidney transplantation was performed in 5 of the 8 patients dialysed for end-stage renal failure. Among 6/16 patients (37%) still alive, 3 belong to the 5 transplanted patients (survival: 3-20 years) and 3 to the anti-TNF-α drugs treated patients; all but one exhibited a low serum amyloid A level.

Conclusions: Suppression of Crohn's disease inflammation potentially leads to the control of amyloid A production, assessed by a decrease of serum amyloid A. Kidney transplantation provides a long survival.

MeSH terms

  • Adolescent
  • Adult
  • Age of Onset
  • Aged
  • Amyloidosis / complications
  • Amyloidosis / mortality
  • Amyloidosis / prevention & control*
  • Crohn Disease / complications*
  • Crohn Disease / mortality
  • Crohn Disease / prevention & control
  • Female
  • Humans
  • Immunosuppressive Agents / therapeutic use
  • Kidney Diseases / complications
  • Kidney Diseases / mortality
  • Kidney Diseases / prevention & control*
  • Kidney Transplantation / mortality
  • Male
  • Middle Aged
  • Retrospective Studies
  • Serum Amyloid A Protein / biosynthesis*
  • Treatment Outcome
  • Tumor Necrosis Factor-alpha / antagonists & inhibitors
  • Young Adult

Substances

  • Immunosuppressive Agents
  • Serum Amyloid A Protein
  • Tumor Necrosis Factor-alpha