Evidence for impaired function of dopaminergic system in Wfs1-deficient mice

Behav Brain Res. 2013 May 1:244:90-9. doi: 10.1016/j.bbr.2013.01.046. Epub 2013 Feb 8.

Abstract

Immunohistological studies suggest abundant expression of Wfs1 protein in neurons and nerve fibers that lie in the vicinity of dopaminergic (DA-ergic) fibers and neurons. Therefore, we sought to characterize the function of DA-ergic system in Wfs1-deficient mice. In wild-type mice, amphetamine, an indirect agonist of DA, caused significant hyperlocomotion and increase in tissue DA levels in the dorsal and ventral striatum. Both effects of amphetamine were significantly blunted in homozygous Wfs1-deficient mice. Motor stimulation caused by apomorphine, a direct DA receptor agonist, was somewhat stronger in Wfs1-deficient mice compared to their wild-type littermates. However, apomorphine caused a similar reduction in levels of DA metabolites (3,4-dihydroxyphenylacetic acid and homovanillic acid) in the dorsal and ventral striatum in all genotypes. Behavioral sensitization to repeated treatment with amphetamine (2.5 mg/kg) was observed in wild-type, but not in Wfs1-deficient mice. The expression of DA transporter gene (Dat) mRNA was significantly lower in the midbrain of male and female homozygous mice compared to wild-type littermates. Altogether, the blunted effects of amphetamine and the reduced gene expression of DA transporter are probably indicative of an impaired functioning of the DA-ergic system in Wfs1-deficient mice.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Amphetamine / pharmacology
  • Animals
  • Apomorphine / pharmacology
  • Central Nervous System Sensitization / physiology
  • Corpus Striatum / drug effects
  • Corpus Striatum / metabolism
  • Corpus Striatum / physiology*
  • Dopamine / metabolism
  • Dopamine Agents / pharmacology
  • Dopamine Plasma Membrane Transport Proteins / metabolism
  • Dopaminergic Neurons / drug effects
  • Dopaminergic Neurons / physiology*
  • Female
  • Gene Expression / drug effects
  • Male
  • Membrane Proteins / deficiency*
  • Membrane Proteins / physiology*
  • Mice
  • Mice, Congenic
  • Motor Activity / drug effects
  • Motor Activity / physiology
  • Receptors, Dopamine D2 / metabolism

Substances

  • Dopamine Agents
  • Dopamine Plasma Membrane Transport Proteins
  • Membrane Proteins
  • Receptors, Dopamine D2
  • wolframin protein
  • Amphetamine
  • Apomorphine
  • Dopamine