Germ-line DICER1 mutations do not make a major contribution to the etiology of familial testicular germ cell tumours

BMC Res Notes. 2013 Apr 1:6:127. doi: 10.1186/1756-0500-6-127.

Abstract

Background: The RNase III enzyme DICER1 plays a central role in maturation of microRNAs. Identification of neoplasia-associated germ-line and somatic mutations in DICER1 indicates that mis-expression of miRNAs in cancer may result from defects in their processing. As part of a recent study of DICER1 RNase III domains in 96 testicular germ cell tumors, a single RNase IIIb domain mutation was identified in a seminoma. To further explore the importance of DICER1 mutations in the etiology of testicular germ cell tumors (TGCT), we studied germ-line DNA samples from 43 probands diagnosed with familial TGCT.

Findings: We carried out High Resolution Melting Curve Analysis of DICER1 exons 2-12, 14-19, 21 and 24-27. All questionable melt curves were subjected to confirmatory Sanger sequencing.Sanger sequencing was used for exons 13, 20, 22 and 23. Intron-exon boundaries were included in all analyses. We identified 12 previously reported single nucleotide polymorphisms and two novel single nucleotide variants. No likely deleterious variants were identified; notably no mutations that were predicted to truncate the protein were identified.

Conclusions: Taken together with previous studies, the findings reported here suggest a very limited role for either germ-line or somatic DICER1 mutations in the etiology of TGCT.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • DEAD-box RNA Helicases / genetics*
  • Exons
  • Germ-Line Mutation*
  • Humans
  • Male
  • MicroRNAs / metabolism
  • Neoplasms, Germ Cell and Embryonal / genetics*
  • Polymorphism, Single Nucleotide
  • Protein Structure, Tertiary
  • Ribonuclease III / genetics*
  • Ribonuclease III / metabolism
  • Seminoma / metabolism
  • Sequence Analysis, DNA
  • Testicular Neoplasms / genetics*

Substances

  • MicroRNAs
  • DICER1 protein, human
  • Ribonuclease III
  • DEAD-box RNA Helicases