XY sex reversal, pontocerebellar hypoplasia and intellectual disability: confirmation of a new syndrome

Am J Med Genet A. 2013 Jul;161A(7):1714-7. doi: 10.1002/ajmg.a.35945. Epub 2013 May 17.

Abstract

We report on a 46,XY female with pontocerebellar hypoplasia and intellectual disability. To our knowledge, this is the fourth reported patient with this constellation and further confirms a rare new syndrome. The condition is probably a single gene disorder with a currently unknown mode of inheritance. The causative gene is likely involved in the normal gonadal sex determination as well as the cerebral and cerebellar formation and function.

Publication types

  • Case Reports

MeSH terms

  • Adolescent
  • Child
  • Female
  • Gonadal Dysgenesis, 46,XY / etiology*
  • Humans
  • Intellectual Disability / genetics*
  • Male
  • Olivopontocerebellar Atrophies / genetics*
  • Pregnancy
  • Syndrome

Supplementary concepts

  • 46, XY female