Progressive cognitive dysfunction in spinocerebellar ataxia type 3

Mov Disord. 2013 Sep;28(10):1435-8. doi: 10.1002/mds.25512. Epub 2013 Jun 4.

Abstract

Background: Although it is well established that there is cognitive dysfunction in spinocerebellar ataxia type 3 (SCA3), it is unknown whether cognition deteriorates with disease progression. We therefore prospectively studied cognitive function in patients with SCA3.

Methods: Eleven patients with SCA3 were assessed using an extensive neuropsychological test battery and retested after 3.5 ± 0.4 years.

Results: In addition to ataxia and motor control, verbal learning and verbal and figural memory deteriorated significantly during the follow-up period. An increase in depressive symptoms was not observed.

Conclusions: The observation that memory and learning abilities deteriorated with disease progression suggests that cognitive dysfunction is an integral part of SCA3. Because the applied tests for memory function did not require motor responses, cognitive decline cannot be attributed to progressive cerebellar ataxia. The deterioration of verbal and figural memory can be explained either by extracerebellar pathology or by disruption of cerebellar-cerebral circuitries.

Keywords: SCA3; ataxia; cerebellum; cognition; follow-up.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Analysis of Variance
  • Cognition Disorders / etiology
  • Cognition Disorders / psychology*
  • Depression / etiology
  • Depression / psychology
  • Disease Progression
  • Female
  • Follow-Up Studies
  • Humans
  • Machado-Joseph Disease / complications
  • Machado-Joseph Disease / genetics
  • Machado-Joseph Disease / psychology*
  • Male
  • Memory / physiology
  • Middle Aged
  • Neurologic Examination
  • Neuropsychological Tests
  • Prospective Studies
  • Psychiatric Status Rating Scales
  • Reaction Time / physiology
  • Verbal Behavior / physiology