Gastrointestinal manifestations in mastocytosis: a study of 83 patients

J Allergy Clin Immunol. 2013 Oct;132(4):866-73.e1-3. doi: 10.1016/j.jaci.2013.05.026. Epub 2013 Jul 26.

Abstract

Background: Mastocytosis is a heterogeneous disease characterized by mast cell accumulation in 1 or more organs. Gastrointestinal manifestations of systemic mastocytosis have been previously studied in small cohorts of patients, and no specific histologic description is available.

Objective: We sought to assess the clinical and pathologic features of gastrointestinal manifestations in patients with mastocytosis.

Methods: Medical history and gastrointestinal symptoms of patients with mastocytosis (n = 83) were compared with those of matched healthy subjects (n = 83) by means of patient questionnaire. Data were analyzed for epidemiologic, clinical, biological, and genetic factors associated with gastrointestinal symptoms for patients with mastocytosis. A comparative analysis of gastrointestinal histology from patients with mastocytosis (n = 23), control subjects with inflammatory bowel disease (n = 17), and healthy subjects (n = 19) was performed.

Results: The following gastrointestinal symptoms occurred more frequently and were more severe in patients with mastocytosis than in healthy subjects: bloating (33% vs 7.2%, P < .0001), abdominal pain (27.3% vs 4.8%, P < .0001), nausea (23% vs 8.4%, P = .02), and diarrhea (33.85% vs 1.2%, P < .0001). Patients with mastocytosis had a significantly higher incidence of personal history of duodenal ulcer (P = .02). Wild-type (WT) c-Kit was associated with diarrhea (P = .03). Specific histologic lesions were present in patients with mastocytosis but were not correlated with clinical symptoms.

Conclusion: Gastrointestinal manifestations in patients with mastocytosis are highly prevalent and often severe. Clinical symptoms do not correspond to histologic findings, are nonspecific, and can simulate irritable bowel syndrome.

Keywords: MC; Mast cell; Mastocytosis; SM; Systemic mastocytosis; WT; Wild-type; c-Kit; gastrointestinal tract; mast cells.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Biopsy
  • Case-Control Studies
  • Diarrhea / metabolism
  • Diarrhea / physiopathology
  • Female
  • Gastrointestinal Diseases / immunology
  • Gastrointestinal Diseases / pathology*
  • Gastrointestinal Diseases / physiopathology*
  • Gastrointestinal Tract / immunology
  • Gastrointestinal Tract / pathology
  • Humans
  • Male
  • Mastocytosis, Systemic / immunology
  • Mastocytosis, Systemic / pathology*
  • Middle Aged
  • Proto-Oncogene Proteins c-kit / metabolism
  • Severity of Illness Index
  • Surveys and Questionnaires

Substances

  • Proto-Oncogene Proteins c-kit