Ultrasound directs a transposase system for durable hepatic gene delivery in mice

Ultrasound Med Biol. 2013 Dec;39(12):2351-61. doi: 10.1016/j.ultrasmedbio.2013.07.002. Epub 2013 Sep 11.

Abstract

Our aim was to evaluate the delivery of transposase-based vectors by ultrasound targeted microbubble destruction (UTMD) in mice. DNA vectors were attached to cationic lipid microbubbles (1-3 μm in diameter), injected intravenously and delivered to the liver by destruction of the carrier bubbles with ultrasound in burst mode at 1.0 MHz, 20-μs pulse duration, 10-Hz pulse repetition frequency and ∼1.3-MPa acoustic peak negative pressure. We evaluated the expression and genomic integration of conventional (pcDNA3) and piggyBac transposase-based (pmGENIE) reporter vectors. In vivo, we observed UTMD-mediated liver-specific expression of pmGENIE for an average of 24 d, compared with 4 d with pcDNA3. Reporter expression was located predominately near blood vessels initially, whereas expression after 3 d was more evenly distributed through the parenchyma of the liver. We confirmed random genomic integration for pmGENIE in vitro; however, integration events for pmGENIE in vivo were targeted to specific areas of chromosome 14. Our results suggest that a combination of UTMD and non-viral DNA transposase vectors can mediate weeks of hepatic-specific gene transfer in vivo, and analyses performed by non-restrictive linear amplification-mediated (nrLAM) polymerase chain reaction, cloning and sequencing identify an unexpected tropism for integration within a specific sequence on chromosome 14 in mice. UTMD delivery of transgenes may be useful for the treatment of hepatic gene deficiency disorders.

Keywords: Hepatic gene therapy; Microbubbles; Site-specific chromosomal integration; Transposase; Ultrasound.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Animals
  • DNA Transposable Elements / genetics
  • Delayed-Action Preparations / administration & dosage
  • Delayed-Action Preparations / chemistry
  • Delayed-Action Preparations / radiation effects*
  • Genetic Vectors / administration & dosage
  • Genetic Vectors / genetics*
  • HEK293 Cells
  • High-Energy Shock Waves
  • Humans
  • Liver / physiology*
  • Male
  • Mice
  • Mice, Inbred C57BL
  • Radiation Dosage
  • Sonication / methods*
  • Transfection / methods*
  • Transposases / genetics*

Substances

  • DNA Transposable Elements
  • Delayed-Action Preparations
  • Transposases