Overexpression of KCNN3 results in sudden cardiac death

Cardiovasc Res. 2014 Feb 1;101(2):326-34. doi: 10.1093/cvr/cvt269. Epub 2013 Dec 1.

Abstract

Background: A recent genome-wide association study identified a susceptibility locus for atrial fibrillation at the KCNN3 gene. Since the KCNN3 gene encodes for a small conductance calcium-activated potassium channel, we hypothesized that overexpression of the SK3 channel increases susceptibility to cardiac arrhythmias.

Methods and results: We characterized the cardiac electrophysiological phenotype of a mouse line with overexpression of the SK3 channel. We generated homozygote (SK3(T/T)) and heterozygote (SK3(+/T)) mice with overexpression of the channel and compared them with wild-type (WT) controls. We observed a high incidence of sudden death among SK3(T/T) mice (7 of 19 SK3(T/T) mice). Ambulatory monitoring demonstrated that sudden death was due to heart block and bradyarrhythmias. SK3(T/T) mice displayed normal body weight, temperature, and cardiac function on echocardiography; however, histological analysis demonstrated that these mice have abnormal atrioventricular node morphology. Optical mapping demonstrated that SK3(T/T) mice have slower ventricular conduction compared with WT controls (SK3(T/T) vs. WT; 0.45 ± 0.04 vs. 0.60 ± 0.09 mm/ms, P = 0.001). Programmed stimulation in 1-month-old SK3(T/T) mice demonstrated inducible atrial arrhythmias (50% of SK3(T/T) vs. 0% of WT mice) and also a shorter atrioventricular nodal refractory period (SK3(T/T) vs. WT; 43 ± 6 vs. 52 ± 9 ms, P = 0.02). Three-month-old SK3(T/T) mice on the other hand displayed a trend towards a more prolonged atrioventricular nodal refractory period (SK3(T/T) vs. WT; 61 ± 1 vs. 52 ± 6 ms, P = 0.06).

Conclusion: Overexpression of the SK3 channel causes an increased risk of sudden death associated with bradyarrhythmias and heart block, possibly due to atrioventricular nodal dysfunction.

Keywords: Arrhythmias; Atrial fibrillation; Heart block; Ion channels; Potassium channel.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Action Potentials
  • Animals
  • Atrioventricular Node / abnormalities
  • Atrioventricular Node / metabolism*
  • Atrioventricular Node / physiopathology
  • Bradycardia / genetics
  • Bradycardia / metabolism*
  • Bradycardia / physiopathology
  • Cardiac Pacing, Artificial
  • Connexin 43 / metabolism
  • Death, Sudden, Cardiac / etiology*
  • Electrocardiography, Ambulatory
  • Genetic Predisposition to Disease
  • Heart Block / genetics
  • Heart Block / metabolism*
  • Heart Block / physiopathology
  • Heterozygote
  • Homozygote
  • Mice
  • Mice, Transgenic
  • Phenotype
  • Small-Conductance Calcium-Activated Potassium Channels / genetics
  • Small-Conductance Calcium-Activated Potassium Channels / metabolism*
  • Time Factors
  • Up-Regulation
  • Voltage-Sensitive Dye Imaging

Substances

  • Connexin 43
  • GJA1 protein, mouse
  • Kcnn3 protein, mouse
  • Small-Conductance Calcium-Activated Potassium Channels