Autosomal dominant inheritance of central centrifugal cicatricial alopecia in black South Africans

J Am Acad Dermatol. 2014 Apr;70(4):679-682.e1. doi: 10.1016/j.jaad.2013.11.035. Epub 2014 Jan 27.

Abstract

Background: Central centrifugal cicatricial alopecia (CCCA) is the commonest type of primary scarring alopecia in women of African descent. Little is currently known about the disease genetics.

Objective: We sought to investigate patterns of inheritance in CCCA and ascertain the contribution of nongenetic factors such as hair-grooming habits to the pathogenesis of the disease.

Methods: Affected individuals with at least 1 available family member were recruited from 2005 through 2012 inclusive for pedigree analysis. CCCA was diagnosed on clinical and histopathological grounds.

Results: Fourteen index African families with 31 immediate family members participated in the initial screening. The female to male ratio was 29:2 with an average age of 50.4 years. All patients displayed histologic features typical for CCCA. Pedigree analysis suggested an autosomal dominant mode of inheritance. Hair-grooming habits were found to markedly influence disease expression.

Limitations: Small number of patients is a limitation.

Conclusion: CCCA can be inherited in an autosomal dominant fashion, with partial penetrance and a strong modifying effect of hairstyling and gender.

Keywords: African; South Africa; black; familial; follicular degeneration syndrome; genetic; hair loss; lymphocytic primary scarring alopecia; scarring alopecia.

Publication types

  • Comparative Study
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Adult
  • Age Distribution
  • Aged
  • Alopecia / ethnology
  • Alopecia / genetics*
  • Alopecia / pathology*
  • Biopsy, Needle
  • Child
  • Chromosome Disorders / genetics
  • Cicatrix / ethnology
  • Cicatrix / genetics
  • Cicatrix / pathology*
  • Cohort Studies
  • Female
  • Genes, Dominant / genetics*
  • Genetic Predisposition to Disease / epidemiology*
  • Humans
  • Immunohistochemistry
  • Incidence
  • Male
  • Middle Aged
  • Pedigree
  • Retrospective Studies
  • Risk Assessment
  • Sex Distribution
  • South Africa / epidemiology
  • Young Adult