[Should we systematically screen for Lynch syndrome in patients with upper urinary tract carcinoma?]

Bull Cancer. 2014 Feb;101(2):144-50. doi: 10.1684/bdc.2014.1896.
[Article in French]

Abstract

Objective: The data describing the urologic extracolonic cancers associated with Lynch syndrome (hereditary non-polyposis colorectal cancer [HNPCC]) are variable. The aim of our study was to establish the frequency of mutations in mismatch repair (MMR) genes in patients with upper urinary tract transitional cell carcinoma (UUT-TCC) and to evaluate the clinical benefits of a systematic screening.

Methods: Specimen blocks were obtained from 146 patients treated for UUT-TCC in our center. Clinicopathological characteristics and survival data of patients were collected (median follow-up = 42.5 months). Immunohistochemistry was performed by tissue microarray (TMA), in order to detect mutations in mismatch repair genes. Results obtained after TMA analysis were confirmed at a molecular level by microsatellite instability (MSI) analysis.

Results: Mutations in mismatch repair genes were detected in seven patients (4.8%) at immunohistochemistry screening, and confirmed by MSI analysis for five of them (3.4%). Clinicopathological characteristics and survival data did not differ significantly in patients with instability compared with patients without. After a median follow-up of 42.5 months, none of them experienced a new HNPCC manifestation.

Conclusion: The frequency of mutations in mismatch repair genes in UUT-TCC was very low, with a good accuracy of immunohistochemistry. Systematic screening should not be proposed in daily practice.

Keywords: Lynch syndrome; immunochemistry; microsatellite instability; upper urinary tract carcinoma.

MeSH terms

  • Adaptor Proteins, Signal Transducing / genetics
  • Adenosine Triphosphatases
  • Adolescent
  • Adult
  • Aged
  • Aged, 80 and over
  • Biomarkers, Tumor / genetics*
  • Carcinoma, Transitional Cell / genetics*
  • Child
  • Child, Preschool
  • Colorectal Neoplasms, Hereditary Nonpolyposis / diagnosis
  • Colorectal Neoplasms, Hereditary Nonpolyposis / genetics*
  • DNA Mismatch Repair / genetics*
  • DNA Repair Enzymes
  • DNA-Binding Proteins / genetics
  • Female
  • Genetic Markers
  • Humans
  • Kidney Neoplasms / genetics*
  • Male
  • Microsatellite Instability*
  • Microsatellite Repeats
  • Middle Aged
  • Mismatch Repair Endonuclease PMS2
  • MutL Protein Homolog 1
  • MutS Homolog 2 Protein / genetics
  • Neoplasm Proteins / genetics*
  • Nuclear Proteins / genetics
  • Retrospective Studies
  • Tissue Array Analysis
  • Ureteral Neoplasms / genetics*
  • Young Adult

Substances

  • Adaptor Proteins, Signal Transducing
  • BAT26 microsatellite DNA
  • Biomarkers, Tumor
  • DNA-Binding Proteins
  • G-T mismatch-binding protein
  • Genetic Markers
  • MLH1 protein, human
  • Neoplasm Proteins
  • Nuclear Proteins
  • Adenosine Triphosphatases
  • PMS2 protein, human
  • Mismatch Repair Endonuclease PMS2
  • MutL Protein Homolog 1
  • MutS Homolog 2 Protein
  • DNA Repair Enzymes