Thoracic duct injury resulting in abnormal newborn screen

J Allergy Clin Immunol Pract. 2013 Nov-Dec;1(6):583-8. doi: 10.1016/j.jaip.2013.09.007. Epub 2013 Oct 31.

Abstract

Measurement of T-cell receptor excision circles (TREC) in neonates has allowed for population-based screening of severe combined immunodeficiency and other disorders associated with T-cell lymphopenia. In addition to primary T-cell lymphopenic disorders, secondary causes of T-cell lymphopenia can be diagnosed with TREC analysis. We discuss the diagnostic evaluation of a patient with normal TREC analysis at birth that became abnormal after cardiac surgery. TREC analysis was performed by the Florida State Laboratory. Diagnostic evaluation and treatment were performed at All Children's Hospital, St Petersburg, Florida. We identified a 38-day-old female patient with thoracic duct injury, which caused chylothorax and chylous ascites diagnosed after an abnormal newborn screen. Chylothorax was secondary to thoracic duct injury after cardiac surgery and led to severe lymphopenia and hypogammaglobulinemia. Thoracic duct ligation led to improved lymphocyte counts and normalization of immunoglobulin levels. Secondary causes of lymphopenia are detected with TREC assay that lead to abnormal newborn screen results. Many secondary causes of lymphopenia can be acquired with normal initial newborn screens that become abnormal over time.

Keywords: Chylothorax; Newborn screen; Severe combined immunodeficiency; T-cell receptor excision circle; Thoracic duct.

Publication types

  • Case Reports
  • Review

MeSH terms

  • Chylothorax / congenital
  • Chylothorax / etiology
  • Chylothorax / surgery
  • Female
  • Humans
  • Infant
  • Infant, Newborn
  • Ligation
  • Lymphocyte Subsets / physiology
  • Neonatal Screening
  • Receptors, Antigen, T-Cell / physiology
  • Severe Combined Immunodeficiency / complications
  • Severe Combined Immunodeficiency / diagnosis*
  • Thoracic Duct / injuries*

Substances

  • Receptors, Antigen, T-Cell

Supplementary concepts

  • Chylothorax, congenital