Fatigue and pruritus at onset identify a more aggressive subset of primary biliary cirrhosis

Liver Int. 2015 Feb;35(2):636-41. doi: 10.1111/liv.12560. Epub 2014 Apr 23.

Abstract

Background & aims: In recent years, primary biliary cirrhosis is mostly diagnosed in patients who are asymptomatic; however, a proportion of cases still present with typical complaints such as fatigue and/or pruritus. We compared biochemical, histological and immunological features of patients with or without fatigue and/or pruritus at onset to see whether the different clinical presentation may eventually impact on disease progression.

Methods: We analysed the Bologna cohort of 216 patients with primary biliary cirrhosis referred to our Centre between 1997 and 2007, according to symptomatic (fatigue and/or pruritus) or asymptomatic presentation. Clinical, biochemical, histological and immunological feature at diagnosis, response to ursodeoxycholic acid and progression of the disorder were compared after a mean follow-up of 81 ± 75 months.

Results: At diagnosis, symptomatic patients were significantly more often women (98.6% vs. 87.2%, P = 0.004), younger (mean age 49 ± 12 vs. 55 ± 12 years, P = 0.003) and with more pronounced biochemical activity, as indicated by higher alkaline phosphatase (mean 2.93 ± 2 vs. 2.12, P = 0.002) and aminotransferase (mean 1.92 ± 1 vs. 1.47 ± 1.27, P = 0.014) levels, whereas histological stage and autoantibody profile were similar. Symptomatic patients were less likely to respond to ursodeoxycholic acid therapy (63% vs. 81%, P = 0.006) and developed more often cirrhosis and its complications (31% vs. 13%, P = 0.004).

Conclusions: Fatigue and/or pruritus at onset identify a subset of patients with primary biliary cirrhosis who preferentially are women, younger, with a particularly active disease, less responsive to ursodeoxycholic acid treatment, and more inclined to evolve to cirrhosis and its complications.

Keywords: antimitochondrial antibodies; biliary; cirrhosis; symptomatic; therapy.

MeSH terms

  • Adult
  • Alkaline Phosphatase / blood
  • Autoantibodies / blood
  • Blotting, Western
  • Cohort Studies
  • Disease Progression
  • Enzyme-Linked Immunosorbent Assay
  • Fatigue / pathology*
  • Female
  • Fluorescent Antibody Technique, Indirect
  • Follow-Up Studies
  • Humans
  • Italy
  • Kaplan-Meier Estimate
  • Liver Cirrhosis, Biliary / classification*
  • Liver Cirrhosis, Biliary / drug therapy*
  • Liver Cirrhosis, Biliary / pathology*
  • Male
  • Middle Aged
  • Pruritus / pathology*
  • Transaminases / blood
  • Ursodeoxycholic Acid / therapeutic use*

Substances

  • Autoantibodies
  • Ursodeoxycholic Acid
  • Transaminases
  • Alkaline Phosphatase