Progressive hepatic mitochondrial dysfunction in premanifest Huntington's disease

Mov Disord. 2014 May;29(6):831-4. doi: 10.1002/mds.25862. Epub 2014 Apr 7.

Abstract

Background: A subclinical, hepatic involvement in manifest and premanifest Huntington's disease (HD) was recently demonstrated by using the (1) (3) C-methionine breath test (MeBT). In this longitudinal pilot study, we investigated whether there is evidence for progressive hepatic mitochondrial dysfunction in premanifest HD.

Methods: The MeBT was performed within a group of 25 well-characterized premanifest HD mutation carriers at baseline and in a 14.5-month follow-up.

Results: The total group of mutation carriers (P = 0.033; Cohen's d = 0.6) and the subgroup of mutation carriers from our PreHD-B subgroup (nearer to disease onset; P = 0.030; Cohen's d = 1.12) revealed a lower amount of exhaled (13) CO2 in the follow-up.

Conclusions: This study demonstrates in vivo progressive, subclinical, hepatic involvement in premanifest HD. Limitations of the study, such as high variance in breath test results, are discussed.

Keywords: liver; methionine; mitochondria; premanifest Huntington's disease.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Disease Progression
  • Female
  • Follow-Up Studies
  • Humans
  • Huntingtin Protein
  • Huntington Disease / complications*
  • Huntington Disease / genetics
  • Liver Diseases / diagnosis
  • Liver Diseases / etiology*
  • Male
  • Middle Aged
  • Mitochondria / pathology
  • Mitochondrial Diseases / etiology*
  • Nerve Tissue Proteins / genetics
  • Statistics as Topic
  • Trinucleotide Repeats / genetics
  • Young Adult

Substances

  • HTT protein, human
  • Huntingtin Protein
  • Nerve Tissue Proteins