Cognitive correlates in amyotrophic lateral sclerosis: a population-based study in Italy

J Neurol Neurosurg Psychiatry. 2015 Feb;86(2):168-73. doi: 10.1136/jnnp-2013-307223. Epub 2014 Apr 25.

Abstract

Background: There is less data available regarding the characteristics of cognitive impairment in patients with amyotrophic lateral sclerosis (ALS) in a population-based series.

Methodology: Patients with ALS incident in Piemonte, Italy, between 2009 and 2011 underwent an extensive neuropsychological battery. Cognitive status was classified as follows: normal cognition, frontotemporal dementia (ALS-FTD), executive cognitive impairment (ALS-ECI), non-executive cognitive impairment (ALS-NECI), behavioural impairment (ALS-Bi), non-classifiable cognitive impairment. We also assessed 127 age-matched and gender-matched controls identified through patients' general practitioners.

Results: Out of the 281 incident patients, 207 (71.9%) underwent the neuropsychological testing; of these, 19 were excluded from the analysis due previous conditions affecting cognition. Ninety-one (49.7%) patients were cognitively normal, 23 (12.6%) had ALS-FTD, 36 (19.7%) ALS-ECI, 10 (5.5%) ALS-NECI, 11 (6.0%) ALS-Bi and 11 (6.0%) non-classifiable cognitive impairment, 1 had comorbid Alzheimer's disease. Patients with ALS-FTD were older, had a lower education level, and had a shorter survival than any other cognitive group. Of the nine cases with C9ORF72 mutation, six had ALS-FTD, two ALS-ECI and one was cognitively normal; one of the five patients with SOD1 mutations and one of the five patients with TARBDP mutations had ALS-Bi.

Conclusions: About 50% of Italian patients with ALS had some degree of cognitive impairment, in keeping with a previous Irish study, despite the largely different genetic background of the two populations. The lower educational attainment in patients with ALS-FTD indicated a possible role of cognitive reserve in ALS-related cognitive impairment. ALS-ECI and ALS-NECI may represent discrete cognitive syndromes in the continuum of ALS and FTD.

Keywords: ALS; DEMENTIA; EPIDEMIOLOGY.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Aged
  • Amyotrophic Lateral Sclerosis / complications
  • Amyotrophic Lateral Sclerosis / epidemiology*
  • Amyotrophic Lateral Sclerosis / genetics
  • Amyotrophic Lateral Sclerosis / psychology*
  • C9orf72 Protein
  • Case-Control Studies
  • Cognition Disorders / classification
  • Cognition Disorders / complications
  • Cognition Disorders / epidemiology*
  • Cognition Disorders / genetics
  • Cognition Disorders / psychology*
  • DNA-Binding Proteins / genetics
  • Female
  • Humans
  • Italy / epidemiology
  • Male
  • Mutation
  • Neuropsychological Tests
  • Proteins / genetics
  • Risk Factors
  • Superoxide Dismutase / genetics
  • Superoxide Dismutase-1
  • Survival Analysis

Substances

  • C9orf72 Protein
  • C9orf72 protein, human
  • DNA-Binding Proteins
  • Proteins
  • SOD1 protein, human
  • Superoxide Dismutase
  • Superoxide Dismutase-1