Deficiency of sphingosine-1-phosphate lyase impairs lysosomal metabolism of the amyloid precursor protein

J Biol Chem. 2014 Jun 13;289(24):16761-72. doi: 10.1074/jbc.M113.535500. Epub 2014 May 7.

Abstract

Progressive accumulation of the amyloid β protein in extracellular plaques is a neuropathological hallmark of Alzheimer disease. Amyloid β is generated during sequential cleavage of the amyloid precursor protein (APP) by β- and γ-secretases. In addition to the proteolytic processing by secretases, APP is also metabolized by lysosomal proteases. Here, we show that accumulation of intracellular sphingosine-1-phosphate (S1P) impairs the metabolism of APP. Cells lacking functional S1P-lyase, which degrades intracellular S1P, strongly accumulate full-length APP and its potentially amyloidogenic C-terminal fragments (CTFs) as compared with cells expressing the functional enzyme. By cell biological and biochemical methods, we demonstrate that intracellular inhibition of S1P-lyase impairs the degradation of APP and CTFs in lysosomal compartments and also decreases the activity of γ-secretase. Interestingly, the strong accumulation of APP and CTFs in S1P-lyase-deficient cells was reversed by selective mobilization of Ca(2+) from the endoplasmic reticulum or lysosomes. Intracellular accumulation of S1P also impairs maturation of cathepsin D and degradation of Lamp-2, indicating a general impairment of lysosomal activity. Together, these data demonstrate that S1P-lyase plays a critical role in the regulation of lysosomal activity and the metabolism of APP.

Keywords: Alzheimer Disease; Amyloid; Amyloid Precursor Protein (APP); Lysosome; Sphingolipid; Sphingosine-1-phosphate (S1P).

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Aldehyde-Lyases / drug effects*
  • Aldehyde-Lyases / genetics
  • Aldehyde-Lyases / metabolism
  • Amyloid Precursor Protein Secretases / metabolism
  • Amyloid beta-Protein Precursor / metabolism*
  • Animals
  • Calcium / metabolism
  • Cathepsin D / metabolism
  • HEK293 Cells
  • Humans
  • Lysophospholipids / metabolism
  • Lysosomal-Associated Membrane Protein 2 / metabolism
  • Lysosomes / metabolism*
  • Mice
  • Proteolysis
  • Sphingosine / analogs & derivatives
  • Sphingosine / metabolism

Substances

  • Amyloid beta-Protein Precursor
  • Lysophospholipids
  • Lysosomal-Associated Membrane Protein 2
  • sphingosine 1-phosphate
  • Amyloid Precursor Protein Secretases
  • Cathepsin D
  • Aldehyde-Lyases
  • sphingosine 1-phosphate lyase (aldolase)
  • Sphingosine
  • Calcium