Multiple sclerosis, solitary sclerosis or something else?

Mult Scler. 2014 Dec;20(14):1819-24. doi: 10.1177/1352458514535129. Epub 2014 May 22.

Abstract

Background: Inflammatory demyelinating diseases of the central nervous system represent a wide spectrum of entities and their classification cannot currently be regarded complete.

Objective: Our aim is to describe a series of patients presenting with progressive myelopathy associated to a single demyelinating lesion of the spinal cord.

Methods: We identified the patients affected by chronic progressive spinal cord dysfunction related to a single spinal cord lesion not satisfying the diagnostic criteria for any of the currently defined diseases.

Results: Seven females and one male were included. The median age at onset of symptoms was 53 years (range 42-68) and the median follow-up was 8 years (range 5-12). Brain and spinal magnetic resonance imaging (MRI) scans detected only one single, circumscribed, T2 hyperintense, non-longitudinally extensive lesion at level of cervico-medullary junction or cervical cord, in the absence of Gadolinium enhancement or swelling. Cerebrospinal fluid (CSF) examination displayed neither oligoclonal bands nor raised IgG index. A response to immunosuppressive agents was observed in some of the patients. Serial control brain and spinal MRI did not reveal accumulation of new lesions.

Conclusion: New entities or variants should be included among the inflammatory demyelinating diseases of the central nervous system, and their characterization may have relevant prognostic and treatment implications.

Keywords: Multiple sclerosis; transverse myelitis.

MeSH terms

  • Adult
  • Aged
  • Cohort Studies
  • Demyelinating Autoimmune Diseases, CNS / pathology
  • Demyelinating Autoimmune Diseases, CNS / physiopathology
  • Female
  • Humans
  • Magnetic Resonance Imaging
  • Male
  • Middle Aged
  • Multiple Sclerosis / pathology*
  • Multiple Sclerosis / physiopathology
  • Myelitis, Transverse / pathology*
  • Myelitis, Transverse / physiopathology
  • Spinal Cord / pathology*
  • Spinal Cord / physiopathology