Surgical management of a hypoplastic distal aortic arch and coarctation of aorta in a patient with Klippel-Feil syndrome, ascending aortic aneurysm and bicuspid aortic valve

Interact Cardiovasc Thorac Surg. 2014 Oct;19(4):708-10. doi: 10.1093/icvts/ivu193. Epub 2014 Jun 30.

Abstract

Klippel-Feil syndrome has been associated with cardiovascular malformations, but only 3 cases have been reported to be associated with aortic coarctation and surgical management is not defined. A 51-year old woman with Klippel-Feil syndrome associated with an aneurysm of the ascending aorta, hypoplastic aortic arch and aortic coarctation at the level of the left subclavian artery presented with shortness of breath 2 years after diagnosis. Imaging identified interim development of a 7.2-cm aneurysm at the level of the aortic coarctation. She underwent surgical repair with a Dacron interposition graft under hypothermic circulatory arrest. She continues to do well 18 months following repair.

Keywords: Aortic coarctation; Hypoplastic distal arch; Klippel–Feil syndrome.

Publication types

  • Case Reports

MeSH terms

  • Abnormalities, Multiple*
  • Aorta, Thoracic / abnormalities
  • Aorta, Thoracic / diagnostic imaging
  • Aorta, Thoracic / surgery*
  • Aortic Aneurysm / diagnosis
  • Aortic Aneurysm / etiology
  • Aortic Aneurysm / surgery*
  • Aortic Coarctation / complications
  • Aortic Coarctation / diagnosis
  • Aortic Coarctation / surgery*
  • Aortic Valve / abnormalities*
  • Aortography / methods
  • Bicuspid Aortic Valve Disease
  • Blood Vessel Prosthesis
  • Blood Vessel Prosthesis Implantation* / instrumentation
  • Female
  • Heart Arrest, Induced
  • Heart Valve Diseases / complications*
  • Heart Valve Diseases / diagnosis
  • Humans
  • Hypothermia, Induced
  • Klippel-Feil Syndrome / complications*
  • Klippel-Feil Syndrome / diagnosis
  • Middle Aged
  • Polyethylene Terephthalates
  • Prosthesis Design
  • Tomography, X-Ray Computed
  • Treatment Outcome

Substances

  • Polyethylene Terephthalates