CYP2W1 is highly expressed in adrenal glands and is positively associated with the response to mitotane in adrenocortical carcinoma

PLoS One. 2014 Aug 21;9(8):e105855. doi: 10.1371/journal.pone.0105855. eCollection 2014.

Abstract

Background: Adrenocortical tumors comprise frequent adenomas (ACA) and rare carcinomas (ACC). Human cytochrome P450 2W1 (CYP2W1) is highly expressed in some cancers holding the potential to activate certain drugs into tumor cytotoxins.

Objective: To investigate the CYP2W1 expression in adrenal samples and its relationship with clinical outcome in ACC.

Material and methods: CYP2W1 expression was investigated by qRT-PCR in 13 normal adrenal glands, 32 ACA, 25 ACC, and 9 different non-adrenal normal tissue samples and by immunohistochemistry in 352 specimens (23 normal adrenal glands, 33 ACA, 239 ACC, 67 non-adrenal normal or neoplastic samples).

Results: CYP2W1 mRNA expression was absent/low in normal non-adrenal tissues, but high in normal and neoplastic adrenal glands (all P<0.01 vs non-adrenal normal tissues). Accordingly, CYP2W1 immunoreactivity was absent/low (H-score 0-1) in 72% of non-adrenal normal tissues, but high (H-score 2-3) in 44% of non-adrenal cancers, in 65% of normal adrenal glands, in 62% of ACAs and in 50% of ACCs (all P<0.001 vs non-adrenal normal tissues), being significantly increased in steroid-secreting compared to non-secreting tumors. In ACC patients treated with mitotane only, high CYP2W1 immunoreactivity adjusted for ENSAT stage was associated with longer overall survival and time to progression (P<0.05 and P<0.01, respectively), and with a better response to therapy both as palliative (response/stable disease in 42% vs 6%, P<0.01) or adjuvant option (absence of disease recurrence in 69% vs 45%, P<0.01).

Conclusion: CYP2W1 is highly expressed in both normal and neoplastic adrenal glands making it a promising tool for targeted therapy in ACC. Furthermore, CYP2W1 may represent a new predictive marker for the response to mitotane treatment.

Publication types

  • Clinical Trial
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adrenal Cortex Neoplasms / drug therapy
  • Adrenal Cortex Neoplasms / enzymology*
  • Adrenal Cortex Neoplasms / pathology
  • Adrenal Glands / enzymology*
  • Adrenal Glands / pathology
  • Adrenocortical Carcinoma / drug therapy
  • Adrenocortical Carcinoma / enzymology*
  • Adrenocortical Carcinoma / pathology
  • Antineoplastic Agents, Hormonal / administration & dosage*
  • Cytochrome P-450 Enzyme System / biosynthesis*
  • Cytochrome P450 Family 2
  • Female
  • Gene Expression Regulation, Enzymologic / drug effects*
  • Gene Expression Regulation, Neoplastic / drug effects*
  • Humans
  • Male
  • Middle Aged
  • Mitotane / administration & dosage*
  • Neoplasm Proteins / biosynthesis*

Substances

  • Antineoplastic Agents, Hormonal
  • Neoplasm Proteins
  • Mitotane
  • Cytochrome P-450 Enzyme System
  • CYP2W1 protein, human
  • Cytochrome P450 Family 2

Grants and funding

This work was supported by a grant from the Wilhelm Sander Foundation (grant number 2012.095.1 to BA). Additional funding was provided by the Deutsche Forschung Gesellschaft (DFG, KR-4371/1-1 to MK and FA 466/4-1 to MF) and also by a grant from the Italian Association for Cancer Research (AIRC, grant number IG/14820/2013 to MP). Publication was funded by the German Research Foundation (DFG) and the University of Wuerzburg in the funding programme Open Access Publishing. The funders had no role in study design, data collection and analysis, decision to publish, or preparation of the manuscript.