SJS/TEN overlap associated with lomefloxacin: case report and molecular typing studies

Dermatology. 2014;229(4):319-23. doi: 10.1159/000365188. Epub 2014 Oct 25.

Abstract

Background: Stevens-Johnson syndrome (SJS) or toxic epidermal necrolysis (TEN) may develop in susceptible patients after administration of different drugs. Only mild cutaneous reactions have been related to lomefloxacin. A correlation between human leucocyte antigen (HLA) and cutaneous adverse reaction has been identified.

Case report: Twenty-four hours after intake of lomefloxacin, a 30-year-old Caucasian woman developed a severe skin reaction with symptoms suggesting SJS/TEN. The fast onset reaction worsened with skin blisters and 20% body surface area skin detachment within 48 h. Burn unit admittance was required; corticosteroids and human immunoglobulins were administered. Complete recovery occurred within 3 months, except for epidermal discoloration. Molecular studies showed a peculiar profile characterized by HLA class I genotype rich of ligands for natural killer cell immunoglobulin-like receptors (KIR) and HLA class II haplotype, HLA-DRB1*03:01,DQB1*02:01, prone to autoimmunity.

Conclusion: While the HLA profile approaches our case to other well-documented drug-induced SJS/TEN, KIR involvement still remains puzzling.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Anti-Bacterial Agents / adverse effects*
  • Female
  • Fluoroquinolones / adverse effects*
  • Genes, MHC Class I
  • Genes, MHC Class II
  • Genotype
  • HLA-G Antigens / genetics
  • Humans
  • Molecular Typing
  • Polymorphism, Genetic
  • Receptors, KIR / genetics
  • Stevens-Johnson Syndrome / etiology
  • Stevens-Johnson Syndrome / genetics*
  • Stevens-Johnson Syndrome / therapy

Substances

  • Anti-Bacterial Agents
  • Fluoroquinolones
  • HLA-G Antigens
  • Receptors, KIR
  • lomefloxacin