Novel antibody associations in immune-mediated necrotising myopathy without inflammation

Ir J Med Sci. 2016 Nov;185(4):941-943. doi: 10.1007/s11845-014-1207-z. Epub 2014 Oct 31.

Abstract

Introduction: The patient presenting with proximal muscle weakness, elevated serum creatinine kinase and myopathic electromyography and biopsy findings has a wide differential diagnosis that includes toxic, autoimmune, paraneoplastic and congenital myopathies. Autoimmune myopathies are important to identify because they may respond to immunosuppressive therapies.

Methods: We describe two cases of immune-mediated necrotizing myopathy each associated with a novel antibody.

Results: Case 1 describes a progressive myopathy in a statin user. Antibodies to 3-hydroxy-3-methyl-glutaryl-coenzyme A reductase were identified and the patient responded to steroid therapy. Case 2 describes an aggressive myopathy associated with antibodies to signal recognition particle. There was no response to steroids. Clinical improvement followed treatment with rituximab and cyclophosphamide.

Conclusion: The identification of myositis-specific antibodies is important because they are associated with distinct clinical phenotypes and may guide the physician in terms of treatment strategies.

Keywords: 3-Hydroxy-3-methyl-glutaryl-CoA reductase inhibitor; Antibody; Immune mediated; Necrotizing myopathy; Signal recognition particle.

Publication types

  • Case Reports
  • Review

MeSH terms

  • Acyl Coenzyme A / immunology
  • Aged
  • Autoantibodies / blood
  • Autoimmune Diseases / immunology*
  • Cyclophosphamide / therapeutic use
  • Humans
  • Hydroxymethylglutaryl-CoA Reductase Inhibitors / therapeutic use
  • Male
  • Middle Aged
  • Muscle, Skeletal / immunology
  • Muscular Diseases / drug therapy
  • Muscular Diseases / immunology*
  • Myositis / immunology
  • Rituximab / therapeutic use
  • Steroids / therapeutic use

Substances

  • Acyl Coenzyme A
  • Autoantibodies
  • Hydroxymethylglutaryl-CoA Reductase Inhibitors
  • Steroids
  • glutaryl-coenzyme A
  • Rituximab
  • Cyclophosphamide