G-quadruplex structures and CpG methylation cause drop-out of the maternal allele in polymerase chain reaction amplification of the imprinted MEST gene promoter

PLoS One. 2014 Dec 1;9(12):e113955. doi: 10.1371/journal.pone.0113955. eCollection 2014.

Abstract

We observed apparent non-Mendelian behaviour of alleles when genotyping a region in a CpG island at the 5' end of the maternally imprinted human MEST isoform. This region contains three single nucleotide polymorphisms (SNPs) in total linkage disequilibrium, such that only two haplotypes occur in the human population. Only one haplotype was detectable in each subject, never both, despite the use of multiple primers and several genotyping methods. We observed that this region contains motifs capable of forming several G-quadruplex structures. Circular dichroism spectroscopy and native polyacrylamide gel electrophoresis confirmed that at least three G-quadruplexes form in vitro in the presence of potassium ions, and one of these structures has a Tm of greater than 99°C in polymerase chain reaction (PCR) buffer. We demonstrate that it is the methylated maternal allele that is always lost during PCR amplification, and that formation of G-quadruplexes and presence of methylated cytosines both contributed to this phenomenon. This observed parent-of-origin specific allelic drop-out has important implications for analysis of imprinted genes in research and diagnostic settings.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Alleles
  • Circular Dichroism
  • CpG Islands*
  • DNA Methylation
  • Depressive Disorder, Major / genetics*
  • G-Quadruplexes
  • Genomic Imprinting
  • Humans
  • In Vitro Techniques / methods
  • Models, Molecular
  • Polymerase Chain Reaction / methods*
  • Potassium / chemistry
  • Promoter Regions, Genetic*
  • Proteins / chemistry*
  • Proteins / genetics*
  • Sequence Analysis, DNA

Substances

  • Proteins
  • mesoderm specific transcript protein
  • Potassium

Grants and funding

This work was supported by the Marsden Fund Council from New Zealand Government funding, administered by the Royal Society of New Zealand. Funding for open access charge was provided by Marsden Fund (11-UOO-175 BMS). The funders had no role in study design, data collection and analysis, decision to publish, or preparation of the manuscript.