Reversal of IgM deficiency following a gluten-free diet in seronegative celiac disease

World J Gastroenterol. 2014 Dec 14;20(46):17686-9. doi: 10.3748/wjg.v20.i46.17686.

Abstract

Selective IgM deficiency (sIGMD) is very rare; it may be associated with celiac disease (CD). We present the case of an 18-year-old man with sIGMD masking seronegative CD. Symptoms included abdominal pain, diarrhea and weight loss. Laboratory tests showed reduced IgM, DQ2-HLA and negative anti-transglutaminase. Villous atrophy and diffuse immature lymphocytes were observed at histology. Tissue transglutaminase mRNA mucosal levels showed a 6-fold increase. The patient was treated with a gluten-free diet (GFD) and six months later the symptoms had disappeared, the villous architecture was restored and mucosal tissue transglutaminase mRNA was comparable to that of healthy subjects. After 1 year of GFD, a complete restoration of normal IgM values was observed and duodenal biopsy showed a reduction of immature lymphocytes and normal appearance of mature immune cells.

Keywords: Gluten-free diet; Selective IgM deficiency; Seronegative celiac disease; Tissue transglutaminase.

Publication types

  • Case Reports
  • Letter

MeSH terms

  • Adolescent
  • Atrophy
  • Autoantibodies / blood*
  • Biomarkers / blood
  • Biopsy
  • Celiac Disease / blood
  • Celiac Disease / diagnosis
  • Celiac Disease / diet therapy*
  • Celiac Disease / genetics
  • Celiac Disease / immunology
  • Diet, Gluten-Free*
  • Duodenum / immunology*
  • Duodenum / pathology
  • GTP-Binding Proteins / genetics
  • GTP-Binding Proteins / immunology*
  • Humans
  • Immunoglobulin M / blood
  • Immunoglobulin M / deficiency*
  • Immunohistochemistry
  • Intestinal Mucosa / immunology*
  • Intestinal Mucosa / pathology
  • Male
  • Protein Glutamine gamma Glutamyltransferase 2
  • RNA, Messenger / analysis
  • Transglutaminases / genetics
  • Transglutaminases / immunology*
  • Treatment Outcome

Substances

  • Autoantibodies
  • Biomarkers
  • Immunoglobulin M
  • RNA, Messenger
  • Protein Glutamine gamma Glutamyltransferase 2
  • Transglutaminases
  • GTP-Binding Proteins