Diagnostic clues and manifesting carriers in fukutin-related protein (FKRP) limb-girdle muscular dystrophy

J Neurol Sci. 2015 Jan 15;348(1-2):266-8. doi: 10.1016/j.jns.2014.12.008. Epub 2014 Dec 9.

Abstract

Mutations in the fukutin-related protein (FKRP) gene are a known cause of autosomal recessive limb-girdle muscular dystrophy. Clinically, patients resemble Becker's muscular dystrophy and generally present in the first two decades of life with a mild, progressive phenotype. Cardiac involvement is variable. Heterozygous carriers are usually clinically unaffected. We report a patient presenting later in life with life-threatening cardiac failure and we describe for the first time clinically manifesting carriers in the family.

Keywords: Cardiac failure; Fukutin-related protein; Late onset; Limb-girdle muscular dystrophy; Manifesting carriers; Muscular dystrophy.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Aged
  • Female
  • Heart Failure / etiology*
  • Heterozygote
  • Humans
  • Membrane Proteins / genetics*
  • Muscular Dystrophies, Limb-Girdle* / complications
  • Muscular Dystrophies, Limb-Girdle* / genetics
  • Muscular Dystrophies, Limb-Girdle* / physiopathology
  • Pedigree

Substances

  • FKTN protein, human
  • Membrane Proteins

Supplementary concepts

  • Limb-girdle muscular dystrophy autosomal recessive