A case of autism spectrum disorder arising from a de novo missense mutation in POGZ

J Hum Genet. 2015 May;60(5):277-9. doi: 10.1038/jhg.2015.13. Epub 2015 Feb 19.

Abstract

Autism spectrum disorder (ASD) is a clinically heterogeneous psychiatric disorder with various genetic backgrounds. Here, we report a novel mutation in the pogo transposable element-derived protein with zinc finger domain gene (POGZ) identified by trio-based whole exome sequencing. To date, a total of seven de novo POGZ mutations in ASD have been reported. POGZ contains a total of five functional domains, and this study reports the first de novo missense mutation in the centromere protein B-like DNA-binding domain. POGZ is highly expressed in the human fetal brain and is involved in mitosis and the regulation of neuronal proliferation. Therefore its loss-of-function or pathogenic missense mutations are likely to be causative of ASD.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Autism Spectrum Disorder / diagnosis*
  • Autism Spectrum Disorder / enzymology
  • Autism Spectrum Disorder / genetics
  • Base Sequence
  • Child, Preschool
  • DNA Mutational Analysis
  • Exome
  • Genetic Association Studies
  • Humans
  • Male
  • Mutation, Missense
  • Transposases / genetics*

Substances

  • POGZ protein, human
  • Transposases