Value of surgical resection in children with high-risk neuroblastoma

Pediatr Blood Cancer. 2015 Sep;62(9):1529-35. doi: 10.1002/pbc.25504. Epub 2015 Mar 23.

Abstract

Background: The value of gross total resection (GTR) for children with high-risk neuroblastoma (NB) is controversial. We hypothesized that patients undergoing GTR would demonstrate improved overall survival (OS) compared those having <GTR.

Methods: Using a single institutional database, we reviewed the medical records of all children with high-risk NB undergoing hematopoietic stem cell transplantation (HSCT) as part of multimodality therapy from 1990 to 2012. Children had received surgical care at multiple institutions (n = 14) prior to HSCT and were divided into two groups based on extent of surgical resection: GTR (no visible or palpable disease at end of operation) and <GTR (no surgery, biopsy only, or subtotal resection). Kaplan-Meier curves and Cox hazards models evaluated differences in overall survival (OS).

Results: One hundred four children underwent HSCT, and 87 (83.6%) had adequate data for analysis. Thirty eight percent had GTR while 62% had <GTR prior to HSCT. There was no significant difference in OS in patients undergoing GTR compared to <GTR (Log rank test: P = 0.49). Post-hoc analysis demonstrated a survival advantage for patients undergoing >90% resection compared to <90% resection (P = 0.008). Multivariable Cox models confirmed these findings with improved survival in children undergoing >90% vs. <90% resection but no difference in GTR vs. <GTR.

Conclusion: Gross total resection prior to HSCT in high-risk NB patients is not associated with improved OS compared to <GTR; however, these results suggest that >90% resection is associated with improved OS compared to less than 90% resection.

Keywords: BMT for malignant conditions; Surgery; neuroblastoma; sickle cell.

Publication types

  • Evaluation Study
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adrenal Gland Neoplasms / drug therapy
  • Adrenal Gland Neoplasms / epidemiology
  • Adrenal Gland Neoplasms / surgery*
  • Adrenal Gland Neoplasms / therapy
  • Adrenalectomy*
  • Antineoplastic Combined Chemotherapy Protocols / therapeutic use
  • Child, Preschool
  • Combined Modality Therapy
  • Female
  • Hematopoietic Stem Cell Transplantation
  • Humans
  • Infant
  • Kaplan-Meier Estimate
  • Male
  • Mediastinal Neoplasms / drug therapy
  • Mediastinal Neoplasms / epidemiology
  • Mediastinal Neoplasms / surgery
  • Mediastinal Neoplasms / therapy
  • Neoadjuvant Therapy
  • Neuroblastoma / drug therapy
  • Neuroblastoma / epidemiology
  • Neuroblastoma / secondary
  • Neuroblastoma / surgery*
  • Neuroblastoma / therapy
  • Peripheral Blood Stem Cell Transplantation
  • Proportional Hazards Models
  • Radiotherapy, Adjuvant
  • Retroperitoneal Neoplasms / drug therapy
  • Retroperitoneal Neoplasms / epidemiology
  • Retroperitoneal Neoplasms / surgery
  • Retroperitoneal Neoplasms / therapy
  • Retrospective Studies
  • Risk
  • Selection Bias
  • Transplantation Conditioning
  • Transplantation, Autologous
  • Treatment Outcome