A First Step toward Personalized Medicine in Osteosarcoma: Pharmacogenetics as Predictive Marker of Outcome after Chemotherapy-Based Treatment

Clin Cancer Res. 2015 Aug 1;21(15):3436-41. doi: 10.1158/1078-0432.CCR-14-2638. Epub 2015 Mar 31.

Abstract

Purpose: Overall survival in patients with osteosarcoma is only 60%. Poor response to chemotherapy is the dominant risk factor for poor survival. Pharmacogenetic research can offer possibilities to optimize treatment and improve outcome. We applied a pathway-based approach to evaluate the cumulative effect of genes involved in the metabolism of cisplatin and doxorubicin in relationship to clinical outcome.

Experimental design: We included 126 patients with osteosarcoma. To comprehensively assess common genetic variation in the 54 genes selected, linkage disequilibrium (LD; r(2) = 0.8)-based tag-single nucleotide polymorphisms (SNP) strategy was used. A final set of 384 SNPs was typed using Illumina Beadarray platform. SNPs significantly associated with 5-year progression-free survival (PFS) were replicated in another 64 patients with osteosarcoma.

Results: We identified five variants in FasL, MSH2, ABCC5, CASP3, and CYP3A4 that were associated with 5-year PFS. Risk stratification based on the combined effects of the risk alleles showed a significant improvement of 5-year PFS. Patients that carried no or only one risk allele had a 5-year PFS of 100% compared with a 5-year PFS of 84.4% for carriers of two or three risk alleles, 66.7% PFS if a patient carried four to five alleles, and a 5-year PFS of 41.8% for patients with >5 risk alleles (P < 0.001).

Conclusions: We identified several genes that showed association with PFS in patients with osteosarcoma. These pharmacogenetic risk factors might be useful to predict treatment outcome and to stratify patients immediately after diagnosis and offer the possibility to improve treatment and outcome.

MeSH terms

  • Adult
  • Aged
  • Caspase 3 / genetics*
  • Cisplatin / administration & dosage
  • Cytochrome P-450 CYP3A / genetics*
  • Disease-Free Survival
  • Doxorubicin / administration & dosage
  • Fas Ligand Protein / genetics*
  • Female
  • Genetic Association Studies
  • Humans
  • Male
  • Middle Aged
  • Multidrug Resistance-Associated Proteins / genetics*
  • MutS Homolog 2 Protein / genetics*
  • Osteosarcoma / drug therapy
  • Osteosarcoma / genetics*
  • Osteosarcoma / pathology
  • Pharmacogenetics*
  • Polymorphism, Single Nucleotide / genetics
  • Precision Medicine
  • Prognosis
  • Treatment Outcome

Substances

  • ABCC5 protein, human
  • FASLG protein, human
  • Fas Ligand Protein
  • Multidrug Resistance-Associated Proteins
  • Doxorubicin
  • Cytochrome P-450 CYP3A
  • CYP3A4 protein, human
  • CASP3 protein, human
  • Caspase 3
  • MSH2 protein, human
  • MutS Homolog 2 Protein
  • Cisplatin