The hidden side of unstable DNA repeats: Mutagenesis at a distance

DNA Repair (Amst). 2015 Aug:32:106-112. doi: 10.1016/j.dnarep.2015.04.020. Epub 2015 May 1.

Abstract

Structure-prone DNA repeats are common components of genomic DNA in all kingdoms of life. In humans, these repeats are linked to genomic instabilities that result in various hereditary disorders, including many cancers. It has long been known that DNA repeats are not only highly polymorphic in length but can also cause chromosomal fragility and stimulate gross chromosomal rearrangements, i.e., deletions, duplications, inversions, translocations and more complex shuffles. More recently, it has become clear that inherently unstable DNA repeats dramatically elevate mutation rates in surrounding DNA segments and that these mutations can occur up to ten kilobases away from the repetitive tract, a phenomenon we call repeat-induced mutagenesis (RIM). This review describes experimental data that led to the discovery and characterization of RIM and discusses the molecular mechanisms that could account for this phenomenon.

Keywords: Cancer; Chromosomal fragility; Contractions; DNA repeats; Expansions; Hereditary Disease; Mutagenesis; Repair; Replication; Transcription.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't
  • Review

MeSH terms

  • Chromosome Aberrations*
  • Chromosome Fragility
  • Chromosomes, Human, Pair 9*
  • DNA / chemistry
  • DNA / metabolism
  • DNA Damage
  • DNA Repair*
  • Frataxin
  • Friedreich Ataxia / genetics*
  • Friedreich Ataxia / metabolism
  • Friedreich Ataxia / pathology
  • Humans
  • Iron-Binding Proteins / genetics*
  • Iron-Binding Proteins / metabolism
  • Mutagenesis*
  • Mutation Rate
  • Trinucleotide Repeat Expansion

Substances

  • Iron-Binding Proteins
  • DNA