Single-molecule analysis reveals widespread structural variation in multiple myeloma

Proc Natl Acad Sci U S A. 2015 Jun 23;112(25):7689-94. doi: 10.1073/pnas.1418577112. Epub 2015 Jun 8.

Abstract

Multiple myeloma (MM), a malignancy of plasma cells, is characterized by widespread genomic heterogeneity and, consequently, differences in disease progression and drug response. Although recent large-scale sequencing studies have greatly improved our understanding of MM genomes, our knowledge about genomic structural variation in MM is attenuated due to the limitations of commonly used sequencing approaches. In this study, we present the application of optical mapping, a single-molecule, whole-genome analysis system, to discover new structural variants in a primary MM genome. Through our analysis, we have identified and characterized widespread structural variation in this tumor genome. Additionally, we describe our efforts toward comprehensive characterization of genome structure and variation by integrating our findings from optical mapping with those from DNA sequencing-based genomic analysis. Finally, by studying this MM genome at two time points during tumor progression, we have demonstrated an increase in mutational burden with tumor progression at all length scales of variation.

Keywords: DNA sequencing; copy number; multiple myeloma; optical mapping; structural variation.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • DNA / genetics
  • DNA Copy Number Variations*
  • Humans
  • Loss of Heterozygosity
  • Multiple Myeloma / genetics*
  • Multiple Myeloma / pathology
  • Polymorphism, Single Nucleotide

Substances

  • DNA

Associated data

  • SRA/SRP058274