Carney complex: an update

Eur J Endocrinol. 2015 Oct;173(4):M85-97. doi: 10.1530/EJE-15-0209. Epub 2015 Jun 30.

Abstract

Carney complex (CNC) is a rare autosomal dominant syndrome, characterized by pigmented lesions of the skin and mucosa, cardiac, cutaneous and other myxomas and multiple endocrine tumors. The disease is caused by inactivating mutations or large deletions of the PRKAR1A gene located at 17q22-24 coding for the regulatory subunit type I alpha of protein kinase A (PKA) gene. Most recently, components of the complex have been associated with defects of other PKA subunits, such as the catalytic subunits PRKACA (adrenal hyperplasia) and PRKACB (pigmented spots, myxomas, pituitary adenomas). In this report, we review CNC, its clinical features, diagnosis, treatment and molecular etiology, including PRKAR1A mutations and the newest on PRKACA and PRKACB defects especially as they pertain to adrenal tumors and Cushing's syndrome.

Publication types

  • Research Support, N.I.H., Intramural
  • Review

MeSH terms

  • Carney Complex / diagnosis
  • Carney Complex / genetics*
  • Carney Complex / therapy
  • Cushing Syndrome / genetics*
  • Cyclic AMP-Dependent Protein Kinase Catalytic Subunits / genetics*
  • Cyclic AMP-Dependent Protein Kinase RIalpha Subunit / genetics*
  • Humans
  • Mutation

Substances

  • Cyclic AMP-Dependent Protein Kinase RIalpha Subunit
  • PRKAR1A protein, human
  • Cyclic AMP-Dependent Protein Kinase Catalytic Subunits
  • PRKACA protein, human
  • PRKACB protein, human