MACULAR HOLES, VITELLIFORM LESIONS, AND MIDPERIPHERAL RETINOSCHISIS IN ALPORT SYNDROME

Retin Cases Brief Rep. 2016 Spring;10(2):109-11. doi: 10.1097/ICB.0000000000000176.

Abstract

Purpose: To describe the retinal findings in two cases of Alport syndrome.

Methods: Observational case series. The clinical findings of the two patients were documented with color fundus photography and high resolution spectral domain optical coherence tomography.

Results: Patient 1 was found to have fleck retinopathy in both eyes, inner retinal thinning in the right eye and a full-thickness macular hole in the left eye. Patient 2 was found to have a full-thickness macular hole in the right eye as well as retinoschisis in the temporal macula in the right eye. The left eye revealed inner retinal thinning involving the fovea, a vitelliform lesion of the temporal macula and midperipheral retinoschisis involving multiple retinal layers.

Conclusion: Retinal abnormalities including fleck retinopathy, retinal thinning, macular holes, retinoschisis, and vitelliform lesions are variably present in Alport syndrome. This is only the second report of a vitelliform lesion in a patient with Alport syndrome and the first report of midperipheral retinoschisis. The array of retinal findings is believed to reflect a dysfunctional Type IV collagen present in the internal limiting membrane and Bruch membrane.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Humans
  • Macula Lutea / pathology*
  • Male
  • Middle Aged
  • Nephritis, Hereditary / complications*
  • Nephritis, Hereditary / diagnosis
  • Retinal Perforations / diagnosis
  • Retinal Perforations / etiology*
  • Retinoschisis / diagnosis
  • Retinoschisis / etiology*
  • Tomography, Optical Coherence / methods*