Pravastatin Therapy and Biomarker Changes in Children and Young Adults with Autosomal Dominant Polycystic Kidney Disease

Clin J Am Soc Nephrol. 2015 Sep 4;10(9):1534-41. doi: 10.2215/CJN.11331114. Epub 2015 Jul 29.

Abstract

Background and objectives: Disease-specific treatment options for autosomal dominant polycystic kidney disease are limited. Clinical intervention early in life is likely to have the greatest effect. In a 3-year randomized double-blind placebo-controlled phase 3 clinical trial, the authors recently showed that pravastatin decreased height-corrected total kidney volume (HtTKV) progression of structural kidney disease over a 3-year period. However, the underlying mechanisms have not been elucidated.

Design, setting, participants, & measurements: Participants were recruited nationally from July 2007 through October 2009. Plasma and urine samples collected at baseline, 18 months, and 36 months from 91 pediatric patients enrolled in the above-mentioned clinical trial were subjected to mass spectrometry-based biomarker analysis. Changes in biomarkers over 3 years were compared between placebo and pravastatin-treated groups. Linear regression was used to evaluate the changes in biomarkers with the percent change in HtTKV over 3 years.

Results: Changes in plasma concentrations of proinflammatory and oxidative stress markers (9- hydroxyoctadecadienoic acid, 13-hydroxyoctadecadienoic acid, and 15-hydroxyeicosatetraenoic acid [HETE]) over 3 years were significantly different between the placebo and pravastatin-treated groups, with the pravastatin group showing a lower rate of biomarker increase. Urinary 8-HETE, 9-HETE, and 11-HETE were positively associated with the changes in HtTKV in the pravastatin group.

Conclusions: Pravastatin therapy diminished the increase of cyclooxygenase- and lipoxygenase-derived plasma lipid mediators. The identified biomarkers and related molecular pathways of inflammation and endothelial dysfunction may present potential targets for monitoring of disease severity and therapeutic intervention of autosomal dominant polycystic kidney disease.

Keywords: angiotensin-converting enzyme inhibitors; autosomal dominant polycystic kidney disease; oxidative stress; pediatric nephrology; statins.

Publication types

  • Clinical Trial, Phase III
  • Randomized Controlled Trial
  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • 12-Hydroxy-5,8,10,14-eicosatetraenoic Acid / blood
  • Adolescent
  • Biomarkers / blood
  • Biomarkers / urine
  • Child
  • Female
  • Humans
  • Hydroxyeicosatetraenoic Acids / blood
  • Hydroxyeicosatetraenoic Acids / urine
  • Hydroxymethylglutaryl-CoA Reductase Inhibitors / therapeutic use*
  • Linoleic Acids / blood
  • Male
  • Organ Size / drug effects
  • Oxidative Stress
  • Polycystic Kidney, Autosomal Dominant / blood*
  • Polycystic Kidney, Autosomal Dominant / drug therapy
  • Polycystic Kidney, Autosomal Dominant / urine*
  • Pravastatin / therapeutic use*
  • Time Factors
  • Young Adult

Substances

  • Biomarkers
  • Hydroxyeicosatetraenoic Acids
  • Hydroxymethylglutaryl-CoA Reductase Inhibitors
  • Linoleic Acids
  • 13-hydroxy-9,11-octadecadienoic acid
  • 12-Hydroxy-5,8,10,14-eicosatetraenoic Acid
  • 11-hydroxy-5,8,12,14-eicosatetraenoic acid
  • 8-hydroxyeicosatetraenoic acid
  • 15-hydroxy-5,8,11,13-eicosatetraenoic acid
  • Pravastatin