Mutation of the BRCA1 SQ-cluster results in aberrant mitosis, reduced homologous recombination, and a compensatory increase in non-homologous end joining

Oncotarget. 2015 Sep 29;6(29):27674-87. doi: 10.18632/oncotarget.4876.

Abstract

Mutations in the breast cancer susceptibility 1 (BRCA1) gene are catalysts for breast and ovarian cancers. Most mutations are associated with the BRCA1 N- and C-terminal domains linked to DNA double-strand break (DSB) repair. However, little is known about the role of the intervening serine-glutamine (SQ) - cluster in the DNA damage response beyond its importance in regulating cell cycle checkpoints. We show that serine-to-alanine alterations at critical residues within the SQ-cluster known to be phosphorylated by ATM and ATR result in reduced homologous recombination repair (HRR) and aberrant mitosis. While a S1387A BRCA1 mutant - previously shown to abrogate S-phase arrest in response to radiation - resulted in only a modest decrease in HRR, S1387A together with an additional alteration, S1423A (BRCA12P), reduced HRR to vector control levels and similar to a quadruple mutant also including S1457A and S1524A (BRCA14P). These effects appeared to be independent of PALB2. Furthermore, we found that BRCA14P promoted a prolonged and struggling HRR late in the cell cycle and shifted DSB repair from HRR to non-homologous end joining which, in the face of irreparable chromosomal damage, resulted in mitotic catastrophe. Altogether, SQ-cluster phosphorylation is critical for allowing adequate time for completing normal HRR prior to mitosis and preventing cells from entering G1 prematurely resulting in gross chromosomal aberrations.

Keywords: DNA damage; DNA repair; cell cycle; phosphorylation; radiation.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Alanine / chemistry
  • Ataxia Telangiectasia Mutated Proteins / metabolism
  • BRCA1 Protein / genetics*
  • Cell Cycle Proteins / metabolism
  • Cell Death
  • Cell Line, Tumor
  • Cell Survival
  • Chromosome Aberrations
  • DNA Breaks, Double-Stranded
  • DNA Damage
  • DNA End-Joining Repair*
  • DNA Repair
  • Glutamine / chemistry*
  • Homologous Recombination*
  • Humans
  • Immunohistochemistry
  • Mitomycin / chemistry
  • Mitosis*
  • Mutation
  • Phosphorylation
  • Protein Structure, Tertiary
  • Recombinant Proteins / genetics
  • S Phase
  • Serine / chemistry*

Substances

  • BRCA1 Protein
  • BRCA1 protein, human
  • Cell Cycle Proteins
  • Recombinant Proteins
  • Glutamine
  • Serine
  • Mitomycin
  • ATM protein, human
  • Ataxia Telangiectasia Mutated Proteins
  • Alanine