Hypothalamic abnormality in patients with inflammatory demyelinating disorders

Int J Neurosci. 2016 Nov;126(11):1036-43. doi: 10.3109/00207454.2015.1114484. Epub 2016 Feb 5.

Abstract

Background: Hypothalamic lesions in neuromyelitis optica (NMO) patients might be more specific for NMO than multiple sclerosis (MS). However, this is controversial.

Objective: To characterize clinical features of patients with inflammatory demyelinating disorders (IDDs) with visible hypothalamic lesions using magnetic resonance imaging (MRI).

Methods: Patients with IDDs (n = 429) were recruited retrospectively.

Results: Of 52 patients with hypothalamic images enrolled, 42 were positive for aquaporin-4 (AQP4) antibodies, including 28 patients with NMO, 6 with recurrent transverse myelitis, 3 with recurrent optic neuritis, and 5 with brainstem and brain syndrome. The remaining 10 patients were anti-AQP4-negative, including 3 with MS, 3 with acute disseminated encephalomyelitis, and 4 with other disorders. In the AQP4-positive group, manifestations, including ataxia, intractable hiccup and nausea, syndrome of inappropriate antidiuretic hormone secretion and encephalopathy were more frequent in those with hypothalamic lesions than those without. Cell counts of cerebrospinal fluid in patients with hypothalamic lesions differed from patients without lesions. Brain MRI abnormalities were more frequent in brainstem and hemisphere of the hypothalamic lesion group.

Conclusions: Hypothalamic lesions were observed frequently in patients with AQP4 antibodies. Clinical manifestations and paraclinical features in AQP4-positive patients with hypothalamic lesions differed from those without lesions.

Keywords: aquaporin-4; hypothalamus; magnetic resonance imaging; neuromyelitis optica.

MeSH terms

  • Adolescent
  • Adult
  • Aged
  • Aquaporin 4 / immunology*
  • Autoantibodies / blood
  • Autoantibodies / cerebrospinal fluid
  • Brain Stem / diagnostic imaging*
  • Child
  • Demyelinating Autoimmune Diseases, CNS* / blood
  • Demyelinating Autoimmune Diseases, CNS* / cerebrospinal fluid
  • Demyelinating Autoimmune Diseases, CNS* / diagnostic imaging
  • Female
  • Humans
  • Hypothalamus / diagnostic imaging*
  • Magnetic Resonance Imaging
  • Male
  • Middle Aged
  • Multiple Sclerosis / blood
  • Multiple Sclerosis / cerebrospinal fluid
  • Multiple Sclerosis / diagnostic imaging
  • Myelitis, Transverse / blood
  • Myelitis, Transverse / cerebrospinal fluid
  • Myelitis, Transverse / diagnostic imaging
  • Neuromyelitis Optica / blood
  • Neuromyelitis Optica / cerebrospinal fluid
  • Neuromyelitis Optica / diagnostic imaging
  • Optic Neuritis* / blood
  • Optic Neuritis* / cerebrospinal fluid
  • Optic Neuritis* / diagnostic imaging
  • Young Adult

Substances

  • AQP4 protein, human
  • Aquaporin 4
  • Autoantibodies