Pseudotumor Cerebri in Acute Promyelocytic Leukemia Patients on Intergroup Protocol 0129: Clinical Description and Recommendations for New Diagnostic Criteria

Clin Lymphoma Myeloma Leuk. 2016 Mar;16(3):146-51. doi: 10.1016/j.clml.2015.11.018. Epub 2015 Nov 22.

Abstract

Background: Multiple randomized trials have demonstrated a benefit for all-trans retinoic acid (ATRA) in patients with acute promyelocytic leukemia (APL). Pseudotumor cerebri (PTC) is an infrequently reported adverse effect of ATRA.

Methods: We examined the incidence, clinical course, and outcomes of patients with APL treated on Intergroup Protocol 0129 (I0129) who developed PTC. This trial evaluated the role of ATRA alone during induction and/or as maintenance therapy.

Results: Of the patients on trial, 240 received ATRA during induction, maintenance, or both; 8 had a clinical suspicion for PTC. Upon review of individual cases, this was felt to be "probable" in 4 patients, "possible" in 1 and "unlikely" in 3 due to lack of diagnostic criteria or presence of a more likely alternate diagnosis.

Conclusions: "Probable" PTC occurred in 1.7% of patients who received ATRA during induction and/or maintenance therapy. In agreement with previous reports, the incidence of PTC in APL patients receiving ATRA was higher in the pediatric population. Here, we discuss the method for diagnosing PTC in the setting of ATRA therapy and management strategies.

Keywords: ATRA; Acute promyelocytic leukemia; All-trans retinoic acid; Neurotoxicity; Pseudotumor cerebri.

Publication types

  • Case Reports

MeSH terms

  • Adolescent
  • Adult
  • Antineoplastic Combined Chemotherapy Protocols / adverse effects*
  • Antineoplastic Combined Chemotherapy Protocols / therapeutic use
  • Child
  • Child, Preschool
  • Female
  • Humans
  • Incidence
  • Induction Chemotherapy
  • Leukemia, Promyelocytic, Acute / complications*
  • Leukemia, Promyelocytic, Acute / drug therapy
  • Maintenance Chemotherapy
  • Male
  • Pseudotumor Cerebri / diagnosis*
  • Pseudotumor Cerebri / epidemiology
  • Pseudotumor Cerebri / etiology*
  • Pseudotumor Cerebri / therapy
  • Randomized Controlled Trials as Topic
  • Treatment Outcome
  • Tretinoin / adverse effects
  • Tretinoin / therapeutic use
  • Young Adult

Substances

  • Tretinoin