Combination of two different homozygote mutations in Pompe disease

Pediatr Int. 2016 Mar;58(3):241-243. doi: 10.1111/ped.12873.

Abstract

Pompe disease (OMIM no 232300) is an autosomal recessive inherited metabolic disorder, caused by glycogen accumulation in the lysosome due to deficiency of the lysosomal acid 03B1-glucosidase enzyme. Here we report the case of an 8-month-old girl of consanguineous Turkish parents, who was diagnosed with the infantile form of Pompe disease. Two different uncommon homozygote mutations (c.32-13 T > G homozygote and c.1856G > A homozygote) were detected. The patient had a more progressive clinical course than expected. We emphasize the rare combination of genetic mutations in this Turkish family with Pompe disease.

Keywords: hypertrophic cardiomyopathy; infantile Pompe disease; novel mutation.

Publication types

  • Case Reports

MeSH terms

  • DNA / genetics*
  • DNA Mutational Analysis
  • Female
  • Genetic Predisposition to Disease*
  • Glycogen Storage Disease Type II / genetics*
  • Homozygote
  • Humans
  • Infant
  • Mutation*
  • Phenotype
  • alpha-Glucosidases / genetics*
  • alpha-Glucosidases / metabolism

Substances

  • DNA
  • alpha-Glucosidases