Monoclonal gammopathy-associated pure red cell aplasia

Br J Haematol. 2016 Jun;173(6):876-83. doi: 10.1111/bjh.14012. Epub 2016 Mar 21.

Abstract

Pure red cell aplasia (PRCA) is a rare disorder characterized by inhibition of erythroid precursors in the bone marrow and normochromic, normocytic anaemia with reticulocytopenia. Among 51 PRCA patients, we identified 12 (24%) patients having monoclonal gammopathy, monoclonal gammopathy of undetermined significance or smouldering multiple myeloma, with presence of monoclonal protein or abnormal serum free light chains and atypical bone marrow features of clonal plasmacytosis, hypercellularity and fibrosis. Thus far, three patients treated with anti-myeloma based therapeutics have responded with reticulocyte recovery and clinical transfusion independence, suggesting plasma cells play a key role in the pathogenesis of this specific monoclonal gammopathy-associated PRCA.

Keywords: anaemia; monoclonal gammopathy of undetermined significance; myeloma; plasmacytosis; pure red cell aplasia.

MeSH terms

  • Adult
  • Aged
  • Bone Marrow / pathology
  • Dexamethasone / therapeutic use
  • Diagnosis, Differential
  • Female
  • Humans
  • Immunoglobulins / blood
  • Lenalidomide
  • Male
  • Middle Aged
  • Multiple Myeloma / diagnosis*
  • Multiple Myeloma / pathology
  • Paraproteinemias / diagnosis*
  • Paraproteinemias / pathology
  • Plasma Cells / physiology
  • Red-Cell Aplasia, Pure / diagnosis*
  • Red-Cell Aplasia, Pure / pathology
  • Reticulocyte Count
  • Reticulocytes / physiology
  • Thalidomide / analogs & derivatives
  • Thalidomide / therapeutic use
  • Young Adult

Substances

  • Immunoglobulins
  • M-proteins (Myeloma)
  • Thalidomide
  • Dexamethasone
  • Lenalidomide