The role of germline alterations in the DNA damage response genes BRIP1 and BRCA2 in melanoma susceptibility

Genes Chromosomes Cancer. 2016 Jul;55(7):601-11. doi: 10.1002/gcc.22363. Epub 2016 May 2.

Abstract

We applied a targeted sequencing approach to identify germline mutations conferring a moderately to highly increased risk of cutaneous and uveal melanoma. Ninety-two high-risk melanoma patients were screened for inherited variation in 120 melanoma candidate genes. Observed gene variants were filtered based on frequency in reference populations, cosegregation with melanoma in families and predicted functional effect. Several novel or rare genetic variants in genes involved in DNA damage response, cell-cycle regulation and transcriptional control were identified in melanoma patients. Among identified genetic alterations was an extremely rare variant (minor allele frequency of 0.00008) in the BRIP1 gene that was found to cosegregate with the melanoma phenotype. We also found a rare nonsense variant in the BRCA2 gene (rs11571833), previously associated with cancer susceptibility but not with melanoma, which showed weak association with melanoma susceptibility in the Swedish population. Our results add to the growing knowledge about genetic factors associated with melanoma susceptibility and also emphasize the role of DNA damage response as an important factor in melanoma etiology. © 2016 Wiley Periodicals, Inc.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Aged
  • Aged, 80 and over
  • BRCA2 Protein / genetics*
  • Case-Control Studies
  • DNA Damage / genetics*
  • DNA, Neoplasm / analysis
  • DNA, Neoplasm / genetics
  • DNA-Binding Proteins / genetics*
  • Fanconi Anemia Complementation Group Proteins
  • Female
  • Follow-Up Studies
  • Genetic Predisposition to Disease*
  • Germ-Line Mutation / genetics*
  • Humans
  • Male
  • Melanoma / genetics*
  • Melanoma / pathology
  • Middle Aged
  • Pedigree
  • Prognosis
  • RNA Helicases / genetics*

Substances

  • BRCA2 Protein
  • BRCA2 protein, human
  • DNA, Neoplasm
  • DNA-Binding Proteins
  • Fanconi Anemia Complementation Group Proteins
  • BRIP1 protein, human
  • RNA Helicases