Non-IgG4-related Multifocal Fibrosclerosis

Intern Med. 2016;55(17):2497-502. doi: 10.2169/internalmedicine.55.6297. Epub 2016 Sep 1.

Abstract

Multifocal fibrosclerosis (MFS), which causes systemic and chronic connective tissue inflammation, has been associated with IgG4 and regarded as an identical entity with "IgG4-related disease (IgG4-RD)". Although a few cases of MFS mimicking IgG4-RD histopathologically, despite the absence of a serum IgG4 elevation and IgG4-positive plasma cell infiltration, have been reported, there is, so far, little information regarding such exceptional cases. We herein demonstrate a case of non-IgG4-related MFS presenting with periaortitis and parotiditis, whose histological findings were consistent with IgG4-RD despite the absence of elevated serum and tissue IgG4 levels.

Publication types

  • Case Reports

MeSH terms

  • Humans
  • Immunoglobulin G / blood*
  • Male
  • Middle Aged
  • Parotitis / complications
  • Retroperitoneal Fibrosis / blood
  • Retroperitoneal Fibrosis / complications
  • Retroperitoneal Fibrosis / congenital*
  • Retroperitoneal Fibrosis / diagnosis

Substances

  • Immunoglobulin G

Supplementary concepts

  • Multifocal fibrosclerosis