Ovarioleukodystrophy due to EIF2B5 mutations

Pract Neurol. 2016 Dec;16(6):496-499. doi: 10.1136/practneurol-2016-001382. Epub 2016 Sep 20.

Abstract

Ovarioleukodystrophy-the co-occurrence of leukodystrophy and premature ovarian failure-is a rare presentation now recognised to be part of the clinical spectrum of vanishing white matter disease. We describe a woman with epilepsy and neuroimaging changes consistent with leukoencephalopathy who presented with non-convulsive status epilepticus after starting hormone replacement therapy in the context of premature ovarian failure. Genetic testing confirmed her to be a compound heterozygote for EIF2B5 mutations; the gene encodes a subunit of eukaryotic translation initiation factor 2B. Mutations in EIF2B1-5 result in vanishing white matter disease. We highlight the importance of ovarian failure as a diagnostic pointer to eukaryotic translation initiation factor 2B (eIF2B)-related ovarioleukodystrophy and present a brief literature review of ovarioleukodystrophy.

Keywords: EIF2B; EPILEPSY; VWM; ovarioleukodystrophy; vanishing white matter.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Eukaryotic Initiation Factor-2B / genetics*
  • Female
  • Humans
  • Leukoencephalopathies / diagnosis
  • Leukoencephalopathies / genetics*
  • Mutation
  • Ovarian Diseases / diagnosis
  • Ovarian Diseases / genetics*
  • Young Adult

Substances

  • EIF2B5 protein, human
  • Eukaryotic Initiation Factor-2B

Supplementary concepts

  • Vanishing White Matter Leukodystrophy with Ovarian Failure