Metachronous anaplastic sarcoma of the kidney and thyroid follicular carcinoma as manifestations of DICER1 abnormalities

Hum Pathol. 2017 Mar:61:205-209. doi: 10.1016/j.humpath.2016.06.024. Epub 2016 Sep 30.

Abstract

Anaplastic sarcoma of the kidney (ASK) is a tumor found in the pediatric age group and shows many histopathological similarities to pleuropulmonary blastoma (PPB). We present a 12-year-old girl diagnosed with ASK and, 3 years later, with thyroid follicular carcinoma (TFC) with DICER1 abnormalities. Germline insertion/deletion (p. G1809_S1814delinsA) and independent somatic mutations (p. E1705K in ASK, p. E1813D in TFC) were identified. All of these abnormalities are in the catalytic domain of RNase IIIb. Single-nucleotide polymorphism genotyping microarray revealed independent copy number alterations (trisomy 8, monosomy 10, loss of 17p, and partial gain of 17q in ASK; trisomy 5 and partial loss of Xq in TFC). The copy number alteration pattern of ASK was similar to the pattern previously reported in PPB. The present case implies that ASK is a renal counterpart of PPB and that ASK with DICER1 abnormalities should be suspected in a broader age group than PPB.

Keywords: Anaplastic sarcoma of the kidney; DICER1; Pleuropulmonary blastoma; RNase III; Thyroid carcinoma.

Publication types

  • Case Reports

MeSH terms

  • Adenocarcinoma, Follicular / enzymology
  • Adenocarcinoma, Follicular / genetics*
  • Adenocarcinoma, Follicular / pathology
  • Adenocarcinoma, Follicular / therapy
  • Biomarkers, Tumor / genetics*
  • Biopsy
  • Child
  • Comparative Genomic Hybridization
  • DEAD-box RNA Helicases / genetics*
  • DNA Copy Number Variations
  • DNA Mutational Analysis
  • Female
  • Gene Dosage
  • Genetic Predisposition to Disease
  • Humans
  • INDEL Mutation*
  • Kidney Neoplasms / enzymology
  • Kidney Neoplasms / genetics*
  • Kidney Neoplasms / pathology
  • Kidney Neoplasms / therapy
  • Mutation, Missense*
  • Neoplasms, Second Primary / enzymology
  • Neoplasms, Second Primary / genetics*
  • Neoplasms, Second Primary / pathology
  • Neoplasms, Second Primary / therapy
  • Phenotype
  • Polymorphism, Single Nucleotide*
  • Ribonuclease III / genetics*
  • Time Factors
  • Treatment Outcome

Substances

  • Biomarkers, Tumor
  • DICER1 protein, human
  • Ribonuclease III
  • DEAD-box RNA Helicases

Supplementary concepts

  • Thyroid cancer, follicular