SDHB mutation status and tumor size but not tumor grade are important predictors of clinical outcome in pheochromocytoma and abdominal paraganglioma

Surgery. 2017 Jan;161(1):230-239. doi: 10.1016/j.surg.2016.05.050. Epub 2016 Nov 10.

Abstract

Background: A staging/prognostic system has long been desired to better categorize pheochromocytoma/paraganglioma which can be very aggressive in the setting of SDHB mutations.

Methods: A retrospective analysis was conducted of clinical characteristics and outcomes including results of genetic testing, tumor recurrence/metastasis, Ki67/MIB1% staining, and tumor mitotic index in patients with pheochromocytoma/paraganglioma.

Results: Patients with SDHB mutation presented at younger age (33.0 years old vs 49.6 years old, P < .001), had increased local recurrence and distant metastases (47.6% vs 9.1%, P < .001, and 56.3% vs 9.1%, P < .001, respectively), and lesser median disease-free interval (89.8 months, 95% confidence interval 36.0-96.4 vs not reached, P < .001). SDHB mutation, greatest tumor diameter, and open operative resection were associated with a greater rate of local recurrence and distant metastases (P < .006 each). SDHB mutation and tumor diameter were independent risk factors for local recurrence (P ≤ .04 each) and metastases. Ki67% and mitotic index were not associated with SDHB mutation (P ≥ .09 each), local recurrence (P = .48, P = .066, respectively), metastases (P ≥ .22 each), or disease-free interval (P ≥ .19 each).

Conclusion: SDHB status and primary tumor size are more predictive of patient outcome than Ki67% or mitotic index and should be part of any clinically relevant, prognostic scoring system.

Publication types

  • Comparative Study
  • Research Support, N.I.H., Intramural

MeSH terms

  • Adrenal Gland Neoplasms / genetics*
  • Adrenal Gland Neoplasms / mortality
  • Adrenal Gland Neoplasms / pathology
  • Adrenal Gland Neoplasms / surgery
  • Adult
  • Aged
  • Biopsy, Needle
  • Cohort Studies
  • Databases, Factual
  • Digestive System Neoplasms / genetics
  • Digestive System Neoplasms / mortality
  • Digestive System Neoplasms / pathology
  • Digestive System Neoplasms / surgery
  • Disease-Free Survival
  • Female
  • Genetic Testing
  • Germ-Line Mutation*
  • Humans
  • Immunohistochemistry
  • Kaplan-Meier Estimate
  • Male
  • Middle Aged
  • Neoplasm Grading
  • Neoplasm Invasiveness / pathology
  • Neoplasm Recurrence, Local / genetics
  • Neoplasm Recurrence, Local / mortality
  • Neoplasm Staging
  • Paraganglioma / genetics*
  • Paraganglioma / mortality
  • Paraganglioma / pathology
  • Paraganglioma / surgery
  • Pheochromocytoma / genetics*
  • Pheochromocytoma / mortality
  • Pheochromocytoma / pathology
  • Pheochromocytoma / surgery
  • Predictive Value of Tests
  • Prognosis
  • Proportional Hazards Models
  • Retrospective Studies
  • Risk Assessment
  • Succinate Dehydrogenase / genetics*
  • Survival Analysis
  • Tumor Burden

Substances

  • SDHB protein, human
  • Succinate Dehydrogenase