Generation of HEXA-deficient hiPSCs from fibroblasts of a Tay-Sachs disease patient

Stem Cell Res. 2016 Sep;17(2):289-291. doi: 10.1016/j.scr.2016.08.010. Epub 2016 Aug 22.

Abstract

Human iPSC line TSD-01-hiPSC was generated from fibroblasts of a patient with infantile Tay-Sachs disease (TSD). The patient is compound heterozygous at the HEXA gene by carrying a 1278insTATC allele and an IVS12+1G>C allele. STEMCCA lentivirus, which expresses OCT4, SOX2, KLF4, and c-MYC from a polycistronic transcript, were used for reprogramming. TSD-01-hiPSC express pluripotency markers such as OCT4, SOX2, NANOG, Tra-1-60, and alkaline phosphatase, and can differentiate into tissues from all the three embryonic germ layers. This TSD patient-derived hiPSC line may serve as a valuable in vitro tool for disease modeling and drug test.

MeSH terms

  • Alleles
  • Animals
  • Base Sequence
  • Cell Differentiation
  • Cell Line
  • Cellular Reprogramming*
  • DNA Mutational Analysis
  • Fibroblasts / cytology
  • Fibroblasts / metabolism
  • Genotype
  • Heterozygote
  • Humans
  • Induced Pluripotent Stem Cells / cytology*
  • Induced Pluripotent Stem Cells / metabolism
  • Induced Pluripotent Stem Cells / transplantation
  • Karyotype
  • Kruppel-Like Factor 4
  • Male
  • Mice
  • Mice, Inbred NOD
  • Mutagenesis, Insertional
  • Tay-Sachs Disease / genetics
  • Tay-Sachs Disease / metabolism
  • Tay-Sachs Disease / pathology*
  • Teratoma / pathology
  • Transcription Factors / genetics
  • Transcription Factors / metabolism
  • Transplantation, Heterologous
  • beta-Hexosaminidase alpha Chain / genetics*

Substances

  • KLF4 protein, human
  • Klf4 protein, mouse
  • Kruppel-Like Factor 4
  • Transcription Factors
  • HEXA protein, human
  • beta-Hexosaminidase alpha Chain